Integration of autography, proteasomal degradation, unfolded protein responce and apoptosis

A single cell has the potential to kill an entire human being. Efforts to cure cancer are limited by survival of individual cancer cells despite immune surveillance and toxic therapies. Understanding the intricate network of pathways that maintain cellular homeostasis and mediate stress response or...

Full description

Saved in:
Bibliographic Details
Published in:Experimental Oncology
Date:2012
Main Authors: Benbrook, D.M., Long, A.
Format: Article
Language:English
Published: Інститут експериментальної патології, онкології і радіобіології ім. Р.Є. Кавецького НАН України 2012
Subjects:
Online Access:https://nasplib.isofts.kiev.ua/handle/123456789/139052
Tags: Add Tag
No Tags, Be the first to tag this record!
Journal Title:Digital Library of Periodicals of National Academy of Sciences of Ukraine
Cite this:Integration of autography, proteasomal degradation, unfolded protein responce and apoptosis / D.M. Benbrook, A. Long // Experimental Oncology. — 2012. — Т. 34, № 3. — С. 286-297. — Бібліогр.: 129 назв. — англ.

Institution

Digital Library of Periodicals of National Academy of Sciences of Ukraine
id nasplib_isofts_kiev_ua-123456789-139052
record_format dspace
spelling Benbrook, D.M.
Long, A.
2018-06-19T18:49:02Z
2018-06-19T18:49:02Z
2012
Integration of autography, proteasomal degradation, unfolded protein responce and apoptosis / D.M. Benbrook, A. Long // Experimental Oncology. — 2012. — Т. 34, № 3. — С. 286-297. — Бібліогр.: 129 назв. — англ.
1812-9269
https://nasplib.isofts.kiev.ua/handle/123456789/139052
A single cell has the potential to kill an entire human being. Efforts to cure cancer are limited by survival of individual cancer cells despite immune surveillance and toxic therapies. Understanding the intricate network of pathways that maintain cellular homeostasis and mediate stress response or default into cell death is critical to the development of strategies to eradicate cancer. Autophagy, proteasomal degradation and the unfolded protein response (UPR) are cellular pathways that degrade and recycle excess or damaged proteins to maintain cellular homeostasis and survival. This review will discuss autophagy and how it is integrated with proteasomal degradation and UPR to govern cell fate through restoration of cellular homeostasis or default into the apoptotic cell death pathway. The first response of autophagy is macroautophagy, which sequesters cytoplasm including organelles inside double-membraned autophagosome vesicles that fuse with lysosomes to degrade and recycle the contents. Ubiquitination patterns on proteins targeted for degradation determine whether adapter proteins will bring them to developing autophagosomes or to proteasomes. Macroautophagy is followed by chaperone-mediated autophagy (CMA), in which Hsc70 (Heat shock cognate 70) selectively binds proteins with exposed KFERQ motifs and pushes them inside lysosomes through the LAMP-2A (Lysosome-associated membrane protein type 2A) receptor. These two processes and the lesser understood microautophagy, which involves direct engulfment of proteins into lysosomes, occur at basal and induced levels. Insufficient proteasome function or ER stress induction of UPR can induce autophagy, which can mitigate damage and stress. If this network is incapable of repairing the damage or overcoming continued stress, the default pathway of apoptosis is engaged to destroy the cell. Induction of macroautophagy by cancer therapeutics has led to clinical trials investigating combinations of HCQ (hydroxychloriquine) suppression of autophagy with apoptosis-inducing agents. Further study of the complex integration of autophagy, proteasomal degradation, UPR and apoptosis is likely to provide additional targets for our fight against cancer. This article is part of a Special Issue entitled “Apoptosis: Four Decades Later”.
en
Інститут експериментальної патології, онкології і радіобіології ім. Р.Є. Кавецького НАН України
Experimental Oncology
Reviews
Integration of autography, proteasomal degradation, unfolded protein responce and apoptosis
Article
published earlier
institution Digital Library of Periodicals of National Academy of Sciences of Ukraine
collection DSpace DC
title Integration of autography, proteasomal degradation, unfolded protein responce and apoptosis
spellingShingle Integration of autography, proteasomal degradation, unfolded protein responce and apoptosis
Benbrook, D.M.
Long, A.
Reviews
title_short Integration of autography, proteasomal degradation, unfolded protein responce and apoptosis
title_full Integration of autography, proteasomal degradation, unfolded protein responce and apoptosis
title_fullStr Integration of autography, proteasomal degradation, unfolded protein responce and apoptosis
title_full_unstemmed Integration of autography, proteasomal degradation, unfolded protein responce and apoptosis
title_sort integration of autography, proteasomal degradation, unfolded protein responce and apoptosis
author Benbrook, D.M.
Long, A.
author_facet Benbrook, D.M.
Long, A.
topic Reviews
topic_facet Reviews
publishDate 2012
language English
container_title Experimental Oncology
publisher Інститут експериментальної патології, онкології і радіобіології ім. Р.Є. Кавецького НАН України
format Article
description A single cell has the potential to kill an entire human being. Efforts to cure cancer are limited by survival of individual cancer cells despite immune surveillance and toxic therapies. Understanding the intricate network of pathways that maintain cellular homeostasis and mediate stress response or default into cell death is critical to the development of strategies to eradicate cancer. Autophagy, proteasomal degradation and the unfolded protein response (UPR) are cellular pathways that degrade and recycle excess or damaged proteins to maintain cellular homeostasis and survival. This review will discuss autophagy and how it is integrated with proteasomal degradation and UPR to govern cell fate through restoration of cellular homeostasis or default into the apoptotic cell death pathway. The first response of autophagy is macroautophagy, which sequesters cytoplasm including organelles inside double-membraned autophagosome vesicles that fuse with lysosomes to degrade and recycle the contents. Ubiquitination patterns on proteins targeted for degradation determine whether adapter proteins will bring them to developing autophagosomes or to proteasomes. Macroautophagy is followed by chaperone-mediated autophagy (CMA), in which Hsc70 (Heat shock cognate 70) selectively binds proteins with exposed KFERQ motifs and pushes them inside lysosomes through the LAMP-2A (Lysosome-associated membrane protein type 2A) receptor. These two processes and the lesser understood microautophagy, which involves direct engulfment of proteins into lysosomes, occur at basal and induced levels. Insufficient proteasome function or ER stress induction of UPR can induce autophagy, which can mitigate damage and stress. If this network is incapable of repairing the damage or overcoming continued stress, the default pathway of apoptosis is engaged to destroy the cell. Induction of macroautophagy by cancer therapeutics has led to clinical trials investigating combinations of HCQ (hydroxychloriquine) suppression of autophagy with apoptosis-inducing agents. Further study of the complex integration of autophagy, proteasomal degradation, UPR and apoptosis is likely to provide additional targets for our fight against cancer. This article is part of a Special Issue entitled “Apoptosis: Four Decades Later”.
issn 1812-9269
url https://nasplib.isofts.kiev.ua/handle/123456789/139052
citation_txt Integration of autography, proteasomal degradation, unfolded protein responce and apoptosis / D.M. Benbrook, A. Long // Experimental Oncology. — 2012. — Т. 34, № 3. — С. 286-297. — Бібліогр.: 129 назв. — англ.
work_keys_str_mv AT benbrookdm integrationofautographyproteasomaldegradationunfoldedproteinresponceandapoptosis
AT longa integrationofautographyproteasomaldegradationunfoldedproteinresponceandapoptosis
first_indexed 2025-11-27T01:36:22Z
last_indexed 2025-11-27T01:36:22Z
_version_ 1850791298286485504
fulltext 286 Experimental Oncology 34, 286–297, 2012 (September) INTEGRATION OF AUTOPHAGY, PROTEASOMAL DEGRADATION, UNFOLDED PROTEIN RESPONSE AND APOPTOSIS D.M. Benbrook1,2,*, A. Long2 1Department of Obstetrics and Gynecology and 2Department of Biochemistry and Molecular Biology University of Oklahoma Health Sciences Center, Oklahoma City, OK 73104, USA A single cell has the potential to kill an entire human being. Efforts to cure cancer are limited by survival of individual cancer cells despite immune surveillance and toxic therapies. Understanding the intricate network of pathways that maintain cellular homeo- stasis and mediate stress response or default into cell death is critical to the development of strategies to eradicate cancer. Au- tophagy, proteasomal degradation and the unfolded protein response (UPR) are cellular pathways that degrade and recycle excess or damaged proteins to maintain cellular homeostasis and survival. This review will discuss autophagy and how it is integrated with proteasomal degradation and UPR to govern cell fate through restoration of cellular homeostasis or default into the apoptotic cell death pathway. The first response of autophagy is macroautophagy, which sequesters cytoplasm including organelles inside double- membraned autophagosome vesicles that fuse with lysosomes to degrade and recycle the contents. Ubiquitination patterns on pro- teins targeted for degradation determine whether adapter proteins will bring them to developing autophagosomes or to proteasomes. Macroautophagy is followed by chaperone-mediated autophagy (CMA), in which Hsc70 (Heat shock cognate 70) selectively binds proteins with exposed KFERQ motifs and pushes them inside lysosomes through the LAMP-2A (Lysosome-associated membrane protein type 2A) receptor. These two processes and the lesser understood microautophagy, which involves direct engulfment of pro- teins into lysosomes, occur at basal and induced levels. Insufficient proteasome function or ER stress induction of UPR can induce autophagy, which can mitigate damage and stress. If this network is incapable of repairing the damage or overcoming continued stress, the default pathway of apoptosis is engaged to destroy the cell. Induction of macroautophagy by cancer therapeutics has led to clinical trials investigating combinations of HCQ (hydroxychloriquine) suppression of autophagy with apoptosis-inducing agents. Further study of the complex integration of autophagy, proteasomal degradation, UPR and apoptosis is likely to provide addi- tional targets for our fight against cancer. This article is part of a Special Issue entitled “Apoptosis: Four Decades Later”. Key Words: autophagy, proteasomal degradation, endoplasmic reticulum stress, unfolded protein response, apoptosis. INTRODUCTION Understanding how cells die is critical knowledge needed for the development of health care strategies to prevent the death of cells in degenerative and acute diseases and to induce the death of diseased cells that can harm the body if not eliminated. Both morphologi- cal and molecular events that occur in dying cells have been characterized and categorized into 13 current modes [37, 68]. More recently, an iron-dependent form of non-apoptotic death termed “ferroptosis” has been described [30]. Autophagy, which was officially identified and named by Christian de Duve in 1963 [22, 59], is formally classified as a form of cell death, how- ever the majority of evidence implicates autophagy as a mechanism to maintain cellular homeostasis and recover from stress, while unequivocal evidence that autophagy causes cell death is rare. The survival func- tion is accomplished through digestion of long-lived or damaged proteins and organelles and release of the components for recycling. The death function is be- lieved to be caused by excessive digestion of cellular components or selective digestion of survival factors over death factors. This review will discuss the integra- tion of autophagy with other cellular processes that maintain homeostasis and mediate stress responses leading to cancer cell survival or death, sometimes through apoptosis, and how these mechanisms are being targeted to improve cancer therapy. For more details on the mechanism of autophagy, readers are directed to several recent reviews [7, 75, 76, 112, 123]. FORMS OF AUTOPHAGY There are three natural processes of autophagy in the cell, MA (macroautophagy), CMA (chaperone- mediated autophagy) and microautophagy. Mac- roautophagy is a natural process in which portions Received: June 15, 2012 *Correspondence: Fax: (405) 271-3874 E-mail: Doris-Benbrook@ouhsc.edu Abbreviations used: AMP — adenosine 5’-monophosphate; AMPK — AMP kinase; ATF — activating transcription factor; ATG — autophagy- related genes; BAG-1 — Bcl-2-associated athanogene 1; Bcl-2 — B-Cell CLL/Lymphoma 2; CHOP — CCAAT/-enhancer- binding protein homologous protein; CMA — chaperone-mediated autophagy; CQ — chloroquine; EF1α — elongation factor 1α; ER — endoplasmic reticulum; ERAD — ER-associated degradation; FIP200 — focal adhesion kinase interacting protein of 200 kD; GADD — growth arrest and DNA damage; Gal3 — galectin-3; GFAP — glial fibrillary acidic protein; GTPases — gua- nosine triphosphatases; HCQ — hydroxychloroquine; HDAC6 — histone deacetylase 6; HLA — human leukocyte antigen; HMGB1 — high mobil- ity group box 1; IGF1 — insulin like growth factor 1; IRE1α — inositol- requiring enzyme 1α; LAMP-2A — lysosome-associated membrane protein type 2A; LC3 — light chain of the microtubule-associated protein 1; MDM2 — murine double minute 2; MEFs — murine embryonic fibro- blasts; MLIV — mucolipidosis Type IV; mTOR — mammalian target of ra- pamycin; NBR1 — neighbor of BRC1; PE — phosphatidylethanoamine; PERK — double-stranded RNA-dependent protein kinase (PKR)-like ER kinase; PI3K — phosphoinositol 3-kinase; PIP3 — PtdIns(3,4,5)P3; PMN — piecemeal microautophagy of the nucleus; PS — phosphoati- dylserine; Rheb — Ras homolog enriched in brain; TRPML1 — transient receptor potential mucolipin-1; TSC — tuberous sclerosis complex; ULK — uncoordinated 51-like kinase; UPR — unfolded protein response; V-ATPase — vacuolar H+ ATPase; Vps — vacuolar protein sorting. Exp Oncol 2012 34, 3, 286–297 INVITED REVIEW Experimental Oncology 34, 286–297, 2012 (September)34, 286–297, 2012 (September) (September) 287 of the cytoplasm, including long-lived proteins and organelles, are sequestered inside double-membraned vesicles called autophagosomes. The autophagosomes eventually fuse with lysosomes to form autophagoly- sosomes where the contents are digested and their components released for recycling within the cells. CMA is driven by Hsc70 (heat shock cognate 70, also called HSPA8 [heat shock protein A8]), which binds specific proteins and transports them directly into the lysosome [76]. In microautophagy, defective molecules or organ- elles are directly engulfed into the lysosomes for degra- dation and recycling of their components [75]. All three forms of autophagy occur at basal levels to maintain the cell, while suprabasal levels are induced by nutrient or oxygen deprivation, endoplasmic reticulum stress, proteasome malfunction or damage caused by drugs or radiation. Most articles refer to macroautophagy as autophagy, however because this article addresses all three forms of autophagy in detail, the term macro- autophagy is used herein to describe the specific pro- cess of autophagosome-mediated recycling. The term autophagy is used in situations where it is feasible that all three forms of autophagy could be actively involved in the process under discussion. MECHANISM, MEASUREMENT AND MANIPULATION OF MACROAUTOPHAGY The production and processing of autophagic ves- icles is divided into 4 steps: 1) initiation, 2) nucleation, 3) maturation and 4) fusion with lysosomes (Fig. 1). These processes are mediated by a series of proteins encoded by autophagy-related genes (ATGs), which were originally characterized in yeast, and are highly conserved in higher eukaryotes [60]. During initiation, de novo synthesis of isolation membranes recruits lipids from several organelles depending on the cell type and stimulus. Electron micrograph documentation of ER located on both sides of isolation membranes, and what appears to be a single bridge connecting the ER to the isola- tion membrane, indicate that this organelle is a source of membrane lipids for the de novo formation of autophagosomes in the cytoplasm [42]. Formation of isolation membranes from the mitochondria ap- pears to be dependent upon PS (phosphatidylserine) transfer from the ER to the mitochondria [41]. The mitochondrial enzyme, PS decarboxylase, converts PS to PE (phosphatidylethanolamine), which is needed for autophagosome formation as described below [113]. Proteins associated with only the outer leaflet of the mitochondrial membrane appear to transfer to the autophagosome, while proteins that traverse the entire mitochondrial membrane are retained in the mi- tochondria [41]. The plasma membrane has also been shown to contribute lipids to the initiation membrane through a process dependent upon the interaction of clatherin on the plasma membrane with Atg16L on the forming autophagosome [100]. An alternative form of macroautophagy shown to occur during fetal development and erythroid maturation derives mem- brane lipids for de novo autophagosome formation from the trans-Golgi and late endosomes [87]. The complex of proteins that mediate initiation con- sists of ULK1 (uncoordinated 51-like kinase 1/Atg1), Atg13 and FIP200 (focal adhesion kinase interacting protein of 200 kD/Atg17). Basal levels of macroau- tophagy are kept in check by mTORC1 (mamma- lian target of rapamycin complex 1) phosphorylation of Atg13 and ULK1, which inhibits ULK1 phosphoryla- tion of FIP200 [12, 38, 44, 49]. The mTORC1 complex is an important component of a network that senses the nutrient state of the cell and accordingly controls the levels of anabolism and catabolism to maintain homeostasis [46] (Fig. 2). High levels of amino acids maintain mTORC1 in an active state by enhancing bind- ing of this complex to regulatory proteins Rag and Rheb (Ras homolog enriched in brain) GTPases (guanosine triphosphatases) [56, 105]. Insulin and IGF1 (insulin like growth factor 1) indirectly induce mTORC1 activity by stimulating class 1 PI3K (phosphoinositol 3-kinase) production of PIP3 (PtdIns(3,4,5)P3), which induces the Akt kinase at the plasma membrane, which in turn activates mTORC1 by inhibiting TSC (tuberous sclero- sis complex) proteins 1 and 2, thereby relieving their repression of Rheb [4, 8]. Low glucose levels or high levels of AMP (adenosine 5’-monophosphate), which indicate low cellular energy status or stress, activate AMPK (AMP-activated protein kinase), which inhibits mTORC1 and stimulates macroautophagy [46, 95]. In summary, high levels of amino acids, insulin and IGF-1 inhibit macroautophagy by inducing the PI3K/ Akt/mTORC1 pathway, while low glucose and high AMP levels induce autophagy by activating the AMPK and repressing mTORC1 activity (Fig. 2). Chemical inhibitors of mTORC1 currently in clinical use or in clini- cal trials, including rapamycin and analogs called Fig. 1. Simplified Illustration of macroautophagy 288 Experimental Oncology 34, 286–297, 2012 (September) rapalogs, such as Everolimus (RAD001), induce macroautophagy and are often used as tools to study autophagy [10, 57]. As discussed below, this induction of macroautophagy interferes with the clinical efficacy of these drugs as anti-cancer agents. Nucleation is controlled by a class III PI3K called Vps34 (vacuolar protein sorting 34) that forms a com- plex with Beclin 1 (Atg6/Vp330), p150 (Vps15) and Atg14L [79]. Production of PIP3 by Vps34 recruits WIPI (WD40 repeat protein Interacting with phosphoInositi- des/Atg18) proteins to the isolation membrane allow- ing recruitment of LC3 (light chain of the microtubule- associated protein 1/ Atg8) and further evolution of the autophagosome [97]. While specific inhibition of class I PI3K stimulates macroautophagy indirectly through downstream Akt/mTOR inhibition, specific inhibi- tion of class III PI3K Vps34 inhibits macroautophagy through reduction of an autophagy-specific PIP3 pool [95]. As discussed below, nucleation can also be inhib- ited by binding of the anti-apoptotic protein Bcl-2 (B- Cell CLL/Lymphoma 2) to Beclin 1 [94]. Two interdependent ubiquitin-like conjugation sys- tems mediate the maturation (elongation, curvature and closure) of the autophagosome. In one system, LC3 is first cleaved by the Atg4 serine protease and then conjugated to PE by the Atg7 and Atg3 enzymes [45]. The unmodified and lipidated forms of LC3 are termed LC3-I and LC3-II, respectively, and can be dis- tinguished by Western blot analysis, a well accepted method to monitor macroautophagy [6]. The second system recruits LC3-II to the isolation membrane by the ubiquitin-like activity of Atg12, which is covalently bound to Atg5 and physically associated with Atg-16L to form a complex [86]. Once the isolation membrane is formed, the Atg-12, -5, -16L complex is released, which affords it’s utilization as a marker of isolation membrane forma- tion [86]. LC3-II on the other hand, remains associated with the autophagosome until fusion with the lyso- some, and the transition of diffuse to punctuate pattern of a transfected LC3-green fluorescent protein fusion protein in the cytoplasm is a commonly used marker of autophagosome formation [6, 86]. Before fusion with the lysosome, ubiquitinated proteins can be brought to the inside of the develop- ing autophagosome by adapter proteins. Proteins are targeted for degradation by E1, E2 and E3 ubiquiti- nases that attach the C-terminal glycine on ubiquitin to the ε-amino group of a lysine residue in the protein being targeted [96]. Multiple molecules of ubiquitin can be added to the same protein as individual com- ponents, and to Lys residues on existing ubiquitins that are already present on the target proteins to form branched chains [119]. Adapter proteins/macro- autophagy receptors called p62, NBR1 (neighbor of BRC1), HDAC6 (histone deacetylase 6) and Alfy bind the ubiquitinated proteins and bring them inside devel- oping autophagosomes [98, 121]. HDAC6 is a micro- tubule associated acetylase that binds to, and utilizes, dynein motors to transport ubiquitinated proteins along microtubles to a structure called the aggresome where they are recognized by developing autophagosomes [53]. As discussed below, the pattern of ubiquitina- tion will determine whether the protein is targeted for autophagic versus proteasomal degradation [98, 121]. The fusion step is mediated by dynein transpor- tation of the autophagosomes along microtubules to fuse with endosomes or lysomes [99]. Microtu- bule disrupting agents, such as taxanes, vinblastine or nocodazole, can prevent the fusion and cause accumulation of autophagic vacuoles [32]. Inhibition of lysosomal acidification by Bafilomycin A, a specific V-ATPase (vacuolar H+ ATPase) inhibitor, or by other lysosomal function inhibitors, CQ (Chloroquine) and HCQ (hydroxychloroquine), also cause accumula- tion of autophagosomes [122, 126]. Upon fusion with the lysosome, the contents are degraded and the components, including amino acids and lipids, are released for re-utilization in cellular metabolism. The TCA (tricarboxylic acid) cycle, which utilizes amino acids for generation of bioenergetic molecules and Fig. 2. Integration of macroautophagy with the regulatory network controlling the maintenance of cellular homeostasis versus apoptosis. The Grp78 under ER stress has two effects, increased Grp78 expression induces autophagic vesicle formation while release of Grp78 inhibition of PERK, EIF2α and ATF6 induce UPR. ATF4 is listed next to PERK because one study indicated that ATF4 stability is responsible for the induction of autophagy. Arrows indicate induction and crossed lines indicate repression. Dashed line indicate hypothesized, not proven, mechanism of Beclin 1 fragment induction of apoptosis. Large open arrow indicates that all three components contribute to CHOP induction Experimental Oncology 34, 286–297, 2012 (September)34, 286–297, 2012 (September) (September) 289 biosynthetic intermediates appears to co-ordinate with macroautophagy through negative feedback of the TCA substrate, pyruvate, on macroautophagy [81]. Al- though not specific for macroautophagy, staining with lysomotropic agents, such as acridine orange, is an ac- ceptable marker for induction of macroautophagy [91]. Electron micrograph evidence of double-membraned vesicles containing cytoplasmic components is a gold standard for the presence of autophagosomes inside cells, while cleared vesicles provide evidence that the autophagic process is proceeding through to diges- tion of the contents and not blocked by lysomotropic agents or other situations. An example of electron micrographic images of autophagosomes and cleared autophagolysomes induced in human ovarian cancer cells by treatment with a novel anti-cancer drug called SHetA2 (NSC 726189) is shown in Fig. 3. INTEGRATION OF THE PROTEASOMAL SYSTEM AND AUTOPHAGY The proteasome partners with autophagy to recycle cellular proteins by digesting single soluble proteins and releasing peptides into the cytoplasm and nucleus to be digested by peptidases, or to be transferred to the ER where they are bound by HLA (human leuko- cyte antigen) proteins and eventually presented on the surface of the cell [25, 64]. Proteasomes are multi- protein complexes made up of an inner 20S cylindri- cal shaped core of subunits that have the proteolytic activity and a 19S regulatory cap of subunits on each end of the core which recognize ubiquitin-conjugated proteins and provide ATPase activity [36]. The protea- some degrades type I (short-lived) and type II (mal- folded/dysfunctional) proteins, whereas autophagy degrades type II and type III (long-lived) proteins [14]. The cellular ubiquitination system specifies whether a protein will be transferred to the protea- some or an autophagosome for recycling. Proteins with attached polyubiquitin chains that are branched on Lys48 have a more closed conformation and are targeted for proteasomal degradation, while proteins with single ubiquitin moieties or polyubiquitin chains that are branched on other Lys residues are targeted to the autophagosomes as described above [98, 121]. Some proteins can be digested by both the proteasome and autophagic vesicles [64]. Degrada- tion of the proteins via the proteasome or autophagy is ultimately determined through competition for bind- ing by adapter proteins, p62 and NBR, which shuttle the proteins to autophagic vesicles, or to p97, which shuttles the proteins to the proteasome [98, 125]. The p62 protein has a higher affinity for the monoubiquiti- nated and Lys63 polyubiquitinated proteins targeted for autophagic degradation, but can also recognize Lys48 polyubiquitin chains targeted for proteasomal degradation, suggesting that p62 can compensate for loss of proteasomal function by bringing Lys48 ubiq- uitylated proteins to the autophagosome when these proteins accumulate during proteasome overload or disfunction [40, 121]. There are several additional levels at which the pro- teasome and autophagy are integrated. Inhibition of the proteasome leads to induction of autophagy [25–27], and induction of autophagy can protect cells from death induced by proteasomal inhibitors [52]. On the other hand, the proteasomal degradation pathway does not appear to compensate for loss of autophagy. Inhibition of early stages of autophagy results in buildup of the p62 adapter, which brings proteins, which would normally be degraded by the proteasome, instead to be accumulated in aggresomes where they can- not be accessed by the proteasomal machinery [63]. Inhibition of autophagy at that last stage of lysosomal degradation by CQ, which does not cause aggresome accumulation, but instead allows the buildup of the ubiquitinated proteins inside lysosomal compartments, also is not compensated by proteasome activity [11]. This unequal relationship between autophagy and pro- teasomal degradation is highlighted by the observations of proteasomes inside closed autophagic vesicles [21]. The induction of autophagy in response to proteasome inhibition is mediated through the unfolded protein response (UPR), which is induced when proteasomal inhibitors cause accumulation of polyubiquitinated proteins leading to ER stress (Fig. 2) [52]. INTEGRATION OF AUTOPHAGY WITH ER STRESS AND UPR ER stress is caused by buildup of unfolded, mis- folded or damaged proteins that exceeds the capacity of chaperones available in the ER to fold them. The UPR sets off a series of events that mitigate this stress and can also lead to induction of autophagy. The observa- tion of ER stress, indicated by swollen ER, occurring in the same cell as autophagic vesicles upon treatment with the SHetA2 anticancer drug, but not upon treat- ment with solvent only, supports the interconnection of these two processes (Fig. 3). An excess of unfolded/ misfolded proteins interferes with the repressive effect of the ER-resident chaperone, Grp78 (glucose regu- lated protein 78, also called HSPA5 [heat shock protein A5] or BiP [Binding immunoglobulin protein]) on three UPR-regulatory proteins called PERK (double-stranded RNA-dependent protein kinase (PKR)-like ER kinase), IRE1α (inositol-requiring enzyme 1α) and ATF6 (Activat- ing transcription factor 6) [93] (Fig. 2). Once released, PERK, IRE1α and ATF6 work in concert to mediate the UPR survival response involving arrest of general pro- tein synthesis, while selected synthesis of chaperone proteins is allowed to continue in order to restore the balance of unfolded proteins/chaperones needed for ER homeostasis [43]. To further reduce the ER load, UPR can cause retrograde translocation of ER proteins to the cytoplasm where they are degraded in the pro- teasome through ERAD (ER associated degradation) [84]. In situations of excess, irreparable or prolonged stress, UPR can transition into apoptosis by upregula- tion of CHOP (CCAAT/-enhancer- binding protein ho- mologous protein) and downstream GADD34 (Growth arrest and DNA damage 34), but in some situations 290 Experimental Oncology 34, 286–297, 2012 (September) autophagy can intervene and prevent cell death by re- moving the accumulated polyubiquitinated proteins and aggregates [29, 90]. ER stress induces autophagy directly through upregulation of Grp78 and through mechanisms downstream of Grp78 release of the three UPR signal transducers (Table 1, Fig. 2). A critical role for Grp78 in the induction of autophagy was de- monstrated with knockdown of Grp78 in normal and cancer cells, which prevented autophagosome formation in response to starvation or in response to inhibition of protein processing with tunicamycin, an inhibitor of N-linked glycosylation [74]. This study also provided evidence for an integral co-dependency of intact ER and autophagy. The massively dilated and disrupted ER and the deficient autophagosome forma- tion induced by Grp78 knockdown were both alleviated by simultaneous knockdown of the XBP-1 transcription factor, a downstream UPR mediator of IRE1α action required for ER expansion [71], suggesting that intact ER is maintained by and/or required for autophagy. The link between Grp78 and autophagy induction occurs downstream of nucleation, as the Grp78 knockdown had no effect on Beclin 1/Vps34 association. The link between the IRE1α arm and upregulation of autophagy is mediated by IRE1α activation of JNK (c-Jun N terminal kinase). Proteasomal inhibition with bortezomib or MG132 induced ER stress and autophagy in colon cancer cells, but not in the pres- ence of siRNA reduction of IRE1α or chemical inhibition of JNK activity, or in IRE1α knockout MEFs (murine em- bryonic fibroblasts) [29]. In this study, the JNK inhibitor had no effect on XBP-1 activation and was equally ef- fective in XBP-1-positive and -negative cells indicating that the UPR induction of autophagy occurs through JNK and not the IRE1α arm of UPR. As discussed above however, the XBP-1 function may be required to maintain the ER in a functional state to support au- tophagic vesicle formation. A similar study conducted in neuroblastoma cells using specific siRNA knock- down of IRE1α, PERK or ATF6, or using a JNK inhibitor, demonstrated that ER stress up-regulated autophagy through a mechanism dependent on IRE1α activation of JNK, but independently of PERK and ATF6 [90]. The ER stress was induced with tunicamycin or thap- sigargin, a chemical that blocks ER calcium uptake by inhibiting ER Ca2+/ATPase. In this model, autophagy protected against cell death as demonstrated by the increase in cell death when autophagy was inhibited by chemical (3-MA [3-methyladenine]) or genetic manipulation (ATG7 siRNA), and inhibited cell death when autophagy was induced by chemical stimulation (rapamycin). The mechanism of autophagy induction downstream of JNK appears to be a result of JNK phos- phorylation of Bcl-2, which releases Bcl-2 repression of Beclin mediation of autophagy [116]. Table 1. Mechanisms of ER stress and UPR induction of autophagy Stressor Cell type Mechanism of autophagy upregulation R Grp78: Tunicamycin, Starvation Embryonal kidney, cervical cancer Downstream of nucleation (Vps34/Beclin1) [74] IRE1α Arm: Bortezomib, MG132 Colon cancer, Prostate cancer IRE1α → JNK → LC3B lipi- dation [29] Tunicamycin, Thapsigargin Neuroblastoma IRE1α → JNK → LC3B lipida- tion → autophagosomes [90] PERK Arm: Misfolded poly- glutamine re- peats Embryonal carci- noma PERK phosphorylation → eIF2α phosphorylation → LC3 lipidation (possibly through increased ATF12 transcription) [65] Bortezomib Pancreatic cancer PERK phosphorylation → eIF2α phosphorylation → ATF4 → Atg 5 and Atg 7 trans- cription [129] Bortezomib Breast cancer Reduction of proteasomal degradation of ATF4 → LC3B transcription [85] PERK, IRE1 α and ATF6 Arms: SPP1 depletion Breast cancer ↑Grp78→ PERK+ IRE1α +ATF6 → LC3B lipidation [72] Indirect: BrefeldinA, Thapsigargin, Tunicamycin Gingival fibroblast p38MAPK → ↑Grp78 and ↑Beclin1 and autophagic ves- icles (possibly through p38 in- hibition of mTORC1) [55] R = reference Fig. 3. Simultaneous induction of ER stress and autophagy. Electron micrographs (X3250 magnification) of the human SK-OV-3 ovar- ian cancer cell line treated with the SHetA2 anti-cancer drug (NSC 721689) for 17 hrs demonstrate normal nuclei (n) swollen ER (SER) and normal ER, double-membraned autophagic vessicles (A) and autophagolysosomes (AL) cleared of their contents, while control cells treated with the same volume of vehicle (dimethylsulfoxide) for 17 hrs do not exhibit SER, A or AL. The lack of clearly identified mitochondria (M) in the treated cells suggests that they may have been digested by autophagy. The inset is enlarged to show the double-membrane on an autophagosome Experimental Oncology 34, 286–297, 2012 (September)34, 286–297, 2012 (September) (September) 291 The link between the PERK arm and upregulation of autophagy is ultimately mediated by ATF4-driven transcriptional upregulation of the ATG genes. Treat- ment of embryonal carcinoma cells with misfolded polyglutamine repeats caused buildup of polyubiq- uitinated protein aggregates and induced LC3 lipi- dation through a mechanism dependent on PERK phosphorylation and activation of eIF2α, and result- ing in autophagic elimination of the aggregates [65]. When the proteasomal inhibitor bortezomib was used in pancreatic cancer cells, the eIF2α led to ac- tivation of ATF4-driven transcription of the ATG5 and ATG7 genes [129]. Activation of eIF2α also was shown to mediate induction of autophagy by starvation and viral infection [110]. Bortezomib treatment of breast cancer cells led to reduction of proteasomal degrada- tion of ATF4, thereby increasing ATF4-mediated LC3B gene transcription [85]. All three of the UPR arms appear to be involved in the induction of autophagy in breast cancer cells caused by accumulation of the sphingolipid metabolite S1P (sphingosine-1-phosphate) phosphatase [72]. In this study, S1P levels were increased by siRNA si- lencing of the SPP1 (S1P phosphatase) responsible for degradation of S1P in the ER. The resulting induc- tion of autophagy was prevented by siRNA silencing of PERK, IRE1α, or ATF6 or a dominant negative PERK mutant. Other upstream inducers of Grp78 and autophagy that have not been characterized for spe- cific UPR arm involvement in the mechanism include p38MAPK (p38 mitogen-activated protein kinase), which likely induces autophagy through inhibition of mTORC1 [55]. The ability of cellular UPR and autophagy respons- es to ER stress to sufficiently mitigate the stress and allow survival is dependent upon the transformation state of the cell and the degree of stress. Although autophagy was induced in both cancer and non-trans- formed cell lines by ER stress inducers tunicamycin, thapsigargin, A23187 (calcium ionophore) or brefeldin A (protein transport inhibitor) and could reduce the buildup of polyubiquitinated proteins, suppression of autophagy using chemical (3-MA) or genetic manip- ulation (siRNA to Beclin 1 or LC3B) reduced cell death in colon and prostate cancer cell lines, but increased cell death in normal non-transformed fibroblast and non-immortalized human colon cell line [28]. The au- thors of this study theorize that the macroautophagy in non-cancer cells may lead to cell death by digest- ing normal by-stander cellular constituents needed for survival. Cancer cells characteristically become growth-independent of these survival factors. The switch between autophagy mediation of cell survival versus death has been shown to be related to the level of stress induced. In normal rat kidney cells, autophagy induced in response to a low dose of cis- platin was required for cell survival, while autophagy induced in response to a high dose of cisplatin was required for cell death [103]. ER stress and Grp78 ap- pear to mediate the induction of autophagy in this model. In a study of ER stress inducers (thapsigargin and tunicamycin) in murine embryonal fibroblasts, low, sublethal doses induced Grp78 expression and acti- vated PERK, IRE1α and ATF6α [104]. Although CHOP was also induced, the upregulation was lost within 24 hrs. Even when CHOP expression was persistently up-regulated, only expression of the down-stream GADD34 correlated with cell death. The authors of this study conclude that differential stability of the Grp78, CHOP and GADD34 mRNA’s and proteins contribute to the ultimate fate of the cell. Similar to the addiction of some cancer cells to cer- tain oncogenes, cancer cells may become dependent upon certain aspects of macroautophagy for cell sur- vival and tumor growth, while defects in macroautoph- agy that accumulate during tumor progression may allow adaptations that prevent apoptosis despite the presence of damaged proteins and organelles [118]. Consistent with this postulate, autophagy has been shown to be critical for K-ras transformation of breast cells [58]. In this model, K-ras induced transformation through a mechanism involving ROS (reactive oxygen species) induction of JNK. As discussed below, inhib- iting autophagy is a current strategy in clinical trials to enhance chemotherapeutic response and overcome resistance of cancer cells. AUTOPHAGY INTEGRATION WITH APOPTOSIS Macroautophagy has been reported to play a role in cell death independently of apoptosis, but it remains unclear if this is a consequence of the severity and/ or extended duration of autophagy, or as a deliberate mechanism of programmed cell death. Autophagic cell death is often described as cell death in the ab- sence of apoptotic caspase activation and presence of autophagic vesicles, but there lacks mechanism that clearly defines autophagic cell death [37]. Whether autophagy contributes to, or reduces, apoptosis in cancer cells is dependent upon the type of cell and the type and duration of stimulus. For instance, autophagy can act as a either a survival or death mechanism within the human SK-OV-3 ovarian cancer cell line, depending on the molecule used to treat the cells [62, 70, 128]. Also, loss of autophagy promotes or prevents fibroblast apoptosis depending on the death stimulus [115]. In the majority of oncology stud- ies however, autophagy appears to play a protective role. For example, in multiple myeloma cells, genetic and chemical inhibition of autophagy enhances induc- tion of apoptosis in vitro and tumor growth inhibition by DNA-damaging drugs, doxorubicin and melphalan in vivo [92]. In rat C6 glioma cells, siRNA silencing of ATG5, ATG7 or ULK1 genes increased apopto- sis caused by cyclosporine A [16]. A recent study screened over 1400 cytotoxic agents for their ability to induce autophagic cell death in the U2Os osteosar- coma cell line [107]. Of the 59 compounds that were validated to truly induce autophagic flux, none of them 292 Experimental Oncology 34, 286–297, 2012 (September) were prevented from inducing cell death when the ATG7 gene critical for autophagy was knocked out. Some fragments of the autophagic machinery are directly involved in the induction of apoptotic cell death through the intrinsic mitochondrial pathway. The transition to apoptosis appears to occur after autopha- gy has been working to save the cell, but activation of specific proteases cleave Atg5 or Beclin 1 releas- ing cleavage products that translocate to the mito- chondria and induce the intrinsic apoptosis pathway (Fig. 2). This direct involvement of Atg5 in apoptosis was demonstrated by enhanced sensitivity of multiple cancer cell types to several cytotoxic chemotherapeu- tic agents upon increased expression of Atg5 protein in vitro and in vivo, while silencing of the ATG5 gene had the opposite effect [127]. In this study, the switch from macroautophagy to apoptosis was mediated by cal- pain cleavage of the Atg5 protein, releasing a truncated Atg5 that translocated to the mitochondria where it bound the anti-apoptotic Bcl-2 molecule, BclXL, thereby relieving BclXL inhibition of the BAX/BAK pore forming ability resulting in cytochrome c release from the mitochondria and caspase activation of apoptosis [127]. The Bcl-2 family of proteins also integrates mac- roautophagy and apoptosis through Beclin 1. Under non-stressed conditions, Bcl-2 binds and sequesters Beclin 1 resulting in suppression of autophagosome formation [94]. Under stressed conditions, JNK be- comes activated and phosphorylates Bcl-2, leading to Bcl-2 degradation and release of Beclin 1 to allow macroautophagy to attempt to recover cellular homeo- stasis [116, 117]. Transition to apoptosis occurs when caspase 3 is activated resulting in a Beclin 1 C-terminal cleavage product that translocates to the mitochondria and enhances apoptosis by releasing pro-apoptotic factors [31, 120]. The known binding of Beclin 1 to the anti-apoptotic BclXL protein is a possible explanation for the induction of apoptosis, similar to what has been reported for Atg5 [88]. Another level of integration between autophagy and apoptosis is controlled by HMGB1 (high mobility group box 1), a nonhistone DNA-binding protein that binds tightly to chromatin of apoptotic cells and is released from necrotic cells [2]. In response to autophagic stimuli, HMGB1 translocates from the nucleus to the cytosol where it binds directly to Beclin 1 causing the release of Bcl-2 and allowing Beclin 1 to increase au- tophagy [111]. Much less is known about the integra- tion of autophagy and programmed necrosis. Although autophagic vesicles have been observed in necrotic cells [2], it is not clear if autophagy is contributing to the cell death in this situation. Based on the ob- servation that combined inhibition of autophagy and apoptosis stimulates necrosis in cancer cells exposed to ischemic conditions, autophagy appears to prevent necrosis [24]. Inconsistent ordering of autophagy and UPR events reported to occur prior to apoptosis suggest that the transition from cell survival to apoptotic death is not linear, but instead driven by an integrated network of events that can eventually tip the balance to sur- vival or death. For example, JNK can be activated upstream of macroautophagy by ER stress, but can also be activated downstream of macroautophagy by etoposide or staurosporine treatment of apoptosis- deficient MEFs [108]. This inconsistency suggests that the pathways are not connected in a linear sequence, but instead integrated at multiple levels. A simplified interpretation may be that autophagic cell death is not a mechanism designed by the cell, but rather a rare consequence of too much autophagy in response to external stimuli, such as chemical reagents or pro- longed stress. The unrestrained autophagy could lead to cell death in the absence of apoptosis by consum- ing the viable cell mass or by upsetting the balance of pro-survival versus pro-apoptotic proteins. This may explain why a definitive molecular mechanism for pro- grammed autophagic cell death has not been defined. TARGETING MACROAUTOPHAGY IN CANCER THERAPY While there is evidence that macroautophagy can suppress the early development of cancer [13], upreg- ulation of basal levels of autophagy in multiple cancers indicate that autophagy primarily drives survival once the tumor has formed [33]. A recently developed meth- od to detect macroautophagy in clinical specimens using immunohistochemistry with an antibody to LC3B demonstrated that punctuate pattern staining of LC3B indicative of macroautophagy significantly correlated with heightened cell proliferation and nuclear grade, invasion and metastasis, and worse outcome [69]. This is of particular significance because multiple anti- cancer agents are known to induce macroautophagy, which could interfere with tumor response (Table 2). Table 2. Anti-cancer agents that induce autophagy Function Name R Alkylating agents Cyclophosphamide, Temozolomide [3, 50] Bcl2 inhibitor GX15-070 [47]* Farnesyltransferase in- hibitor Lonafarnib [47]* Glycolysis inhibitors GX15-070, 2-deoxyglucose [47]* HDAC inhibitors Vorinostat, Sodium butyrate, LAQ824, Panobinostat [47]* Hormone treatments Tamoxifen,Toremifene [47]* Ionizing radiation Cs-137 [91,124] Microtubule inhibitor Vinblastine [101] Monoclonal antibodies Rituximab (to CD20), Panitumumab (to EGF-R) [47]* mTOR inhibitors Sirolimus, Temsirolimus, Everolimus, NV-128 [47]* Natural compounds Arsenic, resveratrol [47]* PARP inhibitor ABT-888 [47]* Proteasome inhibitors Bortezomib, NPI-0052114, Epoxomicin [47]* Topoisomerase poisons Doxorubicin, Campothecin [73, 78] Tyrosine kinase inhibitors Dasatinib, Sorafenib, Imatinib [47]* Vitamin D analog EB1089 [47]* R = references, * Multiple references are provided in this review. Preclinical studies demonstrating a protective role for macroautophagy in response to these therapeutics have translated into multiple clinical trials evalua ting CQ and the derivative HCQ (hydroxychloroquine) inhibition of autophagy in combination with a variety of current cancer treatment strategies. CQ and HCQ are “old drugs” that have been prescribed for malaria Experimental Oncology 34, 286–297, 2012 (September)34, 286–297, 2012 (September) (September) 293 [89], rheumatoid arthritis [66] and HIV [102]. The first reported clinical trial of combining autophagy inhibition with cancer therapy was a single-institution phase III trial in glioblastoma patients treated with conventional radiation and carmustine therapy with or without daily CQ [109]. Although this study was not adequately powered to detect a significant difference in survival, CQ increased overall survival from 11 months in the placebo arm to 24 months in the CQ arm. HCQ is a less toxic version of CQ and the best autophagy inhibitor currently commercially available for clinical trials [39]. Currently there are 84 clinical trials of HCQ listed on the United States Government website (ClinicalTrials.gov), of which 33 are cancer studies, including 15 Phase I, nine Phase I/II, and nine Phase II clinical trials of HCQ in combination with a range of chemotherapeutic agents. In contrast to the sensitization of tumors to che- motherapeutic agents by autophagy inhibition, the sensitivity of tumors to radiation has been shown to be enhanced by induction of autophagy with the mTOR inhibitor everolimus (RAD001) and further enhanced by combined inhibition of apoptosis and induction of autophagy [9, 57]. There are several early phase clinical trials of everolimus or rapamycin in com- bination with radiation therapy for a variety of cancers listed on the ClinicalTrials.gov website. The translation of laboratory-based autophagy studies to clinical trials is based primarily on research of macroautophagy, however there is considerable integration of mac- roautophagy with the other forms of autophagy that could be taken advantage of in this cancer treatment strategy, and that needs to be taken into consideration to fully understand the impact of the interventions and the interpretation of results. MECHANISM AND INTEGRATION OF CHAPERONE-MEDIATED AUTOPHAGY CMA involves the selective degradation of indi- vidual molecules containing an amino acid sequence motif related to KFERQ (Lys-Phe-Glu-Arg-Gln) [27]. CMA activity can be measured in cells by the transition of diffuse to punctuate pattern of a photoconvertible KFERQ-PA-mCherryl reporter protein in transfected cells [61]. It is estimated that at least 30% of cytosolic proteins contain this sequence or a sequence that can be made mimic KFERQ through post-translational modifications [26]. The proteins may have KFERQ lo- cated on their surface for recognition by Hsc70 or this sequence may become exposed upon damage or de- naturing of the protein, or upon separation of the pro- tein with another protein subunit. A single molecular chaperone (Hsc70/HSPA8) appears to mediate the recognition of proteins with exposed KFERQ domains and transporting them to the lysosome [15]. At the lysosome, Hsc70 binds LAMP-2A (Lysosome-asso- ciated membrane protein type 2A), and interacts with a complex of other chaperones to unfold the trans- ported protein and push it through LAMP-2A to an- other molecule of Hsc70 waiting inside the lysosome [1]. Increased expression of LAMP2A and lysosomal Hsc70 correlate with CMA activity and are accepted markers of CMA [18, 19]. Hsc70 binds and hydrolyzes ATP in order to generate the energy required for this process, and the ADP-bound form of Hsc70 has the highest affinity for KFERQ proteins [48]. The proteins working with Hsc70 at the surface of the lysosome have unique functions. Hsp40 activates Hsc70 ATPase activity to increase affinity for protein substrates, Hip (heat shock protein 70 interacting protein) facilitates the assembly of the various proteins in the complex, cdc48 (cell division cycle 48) stimulates the activity of this protein complex, and Bag-1 (Bcl-2-associated athanogene 1) acts as a nucleotide exchange factor that stimulates substrate release [76]. The stability of Hsc70 inside the lysosome is tightly controlled by the pH of the lumen, which, if altered, could denature Hsc70 and make it susceptible to lysosomal proteases [19]. LAMP-2A also works as a complex with EF1α (elongation factor 1 α) to form a complex with GFAP (glial fibrillary acidic protein) that can be negatively regulated by GTP, which causes dissociation of the complex subunits [5]. CMA is a second line response to cell starvation [7]. Macroautophagy is the first line response to nutrient deprivation with maximal activity around 6 hours, fol- lowed by a gradual reduction [35, 83]. There appears to be mutual inhibition between macroautophagy and CMA, as CMA does not increase to suprabasal levels until the reduction of macroautophagy 6 to 8 hours after initiation of starvation [7]. Maximal CMA occurs 24 hours after initiation of starvation and continues for at least 3 days [20]. Although inhibition of macro- autophagy or CMA can lead to upregulation of each other, the compensation is incomplete, as CMA cannot degrade organelles and macroautophagy cannot com- pensate for the selectivity of CMA. Inhibition of CMA by blocking expression of LAMP-2A in fibroblasts resulted in increased macroautophagy, however this compensatory action did not alleviate the increased sensitivity of CMA-deficient cells to stress [83]. In- hibition of macroautophagy with type III PI3K inhibi- tors (3-3-MA, wortmannin or LY294002) or activation of macroautophagy with rapamycin, had no effect on CMA [35], however macroautophagy-deficient cells caused by genetic deletion of ATG5 exhibit up- regulation of both basal and induced CMA through different mechanisms [51]. Although there is little evidence to document direct integration of CMA with ER stress or UPR, integration of CMA with proteasomal degradation is indicated by the selective degradation of proteasomal catalytic core subunits by CMA [21]. Deregulated CMA has been shown to cause mul- tiple diseases including MLIV (mucolipidosis Type IV), which is caused by defects in TRPML1 (transient receptor potential mucolipin-1) leading to ineffec- tive docking with Hsc70 inside the lysosome [114], glaucoma and other diseases related to ineffective Hsc70 transport of proteins along neuronal axons [39]. In cancer, levels of the MDM2 (murine double minute 294 Experimental Oncology 34, 286–297, 2012 (September) 2) regulator of the p53 tumor suppressor protein and the Gal3 (Galectin-3) oncogenic protein, and likely multiple other oncongenes and tumor suppressor genes, are controlled by CMA [77, 80]. A recent study demonstrated that inhibition of constitutively upregu- lated CMA by silencing Lamp-2A expression caused increased p53 levels resulting in reduced proliferation and altered metabolism in human lung cancer cells in vitro and reduced tumor growth and metastases in vivo, indicating that CMA is a relevant target for anti-cancer therapy [61]. MICROAUTOPHAGY Although microautophagy was originally described by de Duve and Wattiauz in 1963, the term was not coined until 1983 [23]. While much less well chara- cterized than macroautophagy and CMA, studies of microautophagy have led to the delineation of 5 se- quential steps that mediate microautophagy, namely: invagination, vesicle formation, vesicle expansion, vesicle scission and vesicle degradation and recycling [75]. The first step of invagination is an ATP-depen- dent process that occurs at areas of the lysosomal membrane with low concentrations of transmem- brane proteins and that develops as tubes filled with cytoplasmic components, in contrast to the shapes of other types of lysosomal invaginations [82, 106]. The subsequent processes are mediated by mTOR regulated ubiquitin-like systems, LC3 lipidation and other Atg machinery similar to that discussed above for macroautophagy [75]. Selective microautophagy degradation of mitochondria (micromitophagy), the nucleus (PMN [piecemeal microautophagy of the nu- cleus]) and peroxisomes (micropexophagy) have been described [34, 54, 67]. Similar to macroautophagy and CMA, microautophagy occurs at basal levels and can be induced by nitrogen starvation or mitochon- drial damage, however in contrast to the antagonism of macroautophagy with CMA, microautophagy ap- pears to work synergistically with the other two forms of autophagy [17]. Although primarily characterized in yeast, defects in microautophagy have been linked to a number of human diseases, however a direct link with cancer has not been identified [75]. CONCLUSIONS Are current definitions of pathways and modes of cell stress response, survival and death limiting our ability to comprehend the dynamic cell? Models are useful, but can introduce bias into our comprehension. This review has described multiple levels of integration between various pathways that can maintain cellular homeostasis or default into apoptosis. Upon stress to the system, the ultimate consequence of cell sur- vival or death depends on balance of events linked at multiple network connections, similar to a hanging mobile. In this model, failure to balance the weights of proteasomal degradation, UPR and autophagy against apoptosis and other forms of cell death, such as programmed necrosis, can lead to excessive au- tophagy consuming the viable cell mass or to the relief of inhibition of the default apoptosis pathway that is al- ways present and waiting for relief of inhibition to kill the cell. The detailed molecular interactions described in this review provide information on the nodes of this complex network that can be manipulated to control the network in development of strategies to induce apoptosis in cancer cells without harming normal cells. REFERENCES 1. Agarraberes FA, Terlecky SR, Dice JF. An intralyso- somal hsp70 is required for a selective pathway of lysosomal protein degradation. J Cell Biol 1997; 137: 825–34. 2. Amaravadi RK, Thompson CB. The roles of therapy- induced autophagy and necrosis in cancer treatment. Clin Cancer Res 2007; 13: 7271–9. 3. Amaravadi RK, Yu D, Lum JJ, et al. Autophagy inhibi- tion enhances therapy-induced apoptosis in a Myc-induced model of lymphoma. J Clin Invest 2007; 117: 326–36. 4. Avruch J, Hara K, Lin Y, et al. Insulin and amino-acid regulation of mTOR signaling and kinase activity through the Rheb GTPase. Oncogene 2006; 25: 6361–72. 5. Bandyopadhyay U, Sridhar S, Kaushik S, et al. Identi- fication of regulators of chaperone-mediated autophagy. Mol Cell 2010; 39: 535–47. 6. Barth S, Glick D, Macleod KF. Autophagy: assays and artifacts. J Pathol 2010; 221: 117–24. 7. Bejarano E, Cuervo AM. Chaperone-mediated au- tophagy. Proc Am Thorac Soc 2010; 7: 29–39. 8. Benbrook DM, Masamha CP. The pro-survival function of Akt kinase can be overridden or altered to contribute to induc- tion of apoptosis. Curr Cancer Drug Targets 2011; 11: 586–99. 9. Cao C, Subhawong T, Albert JM, et al. Inhibition of mammalian target of rapamycin or apoptotic pathway induces autophagy and radiosensitizes PTEN null prostate cancer cells. Cancer Res 2006; 66: 10040–7. 10. Carew J, Kelly K, Nawrocki S. Mechanisms of mTOR in- hibitor resistance in cancer therapy. Target Oncol 2011; 6: 17–27. 11. Carew JS, Medina EC, Esquivel JA 2nd, et al. Autophagy inhibition enhances vorinostat-induced apoptosis via ubiquiti- nated protein accumulation. J Cell Mol Med 2010; 14: 2448–59. 12. Chan EY. mTORC1 phosphorylates the ULK1-mAtg13- FIP200 autophagy regulatory complex. Sci Signal 2009; 2: pe51. 13. Chen N, Karantza-Wadsworth V. Role and regula- tion of autophagy in cancer. Biochim Biophys Acta 2009; 1793: 1516–23. 14. Chen X, Yin XM. Coordination of autophagy and the proteasome in resolving endoplasmic reticulum stress. Vet Pathol 2011; 48: 245–53. 15. Chiang HL, Terlecky SR, Plant CP, Dice JF. A role for a 70-kilodalton heat shock protein in lysosomal degradation of intracellular proteins. Science 1989; 246: 382–5. 16. Ciechomska IA, Gabrusiewicz K, Szczepankiewicz AA, Kaminska B. Endoplasmic reticulum stress triggers autophagy in malignant glioma cells undergoing cyclosporine A-induced cell death. Oncogene 2012 [Epub ahead of print]. 17. Cuervo AM. Autophagy: many paths to the same end. Mol Cell Biochem 2004; 263: 55–72. 18. Cuervo AM, Dice JF. Regulation of lamp2a levels in the lysosomal membrane. Traffic 2000; 1: 570–83. 19. Cuervo AM, Dice JF, Knecht E. A population of rat liver lysosomes responsible for the selective uptake and degradation of cytosolic proteins. J Biol Chem 1997; 272: 5606–15. 20. Cuervo AM, Knecht E, Terlecky SR, Dice JF. Activa- tion of a selective pathway of lysosomal proteolysis in rat liver by prolonged starvation. Am J Physiol 1995; 269: C1200–8. Experimental Oncology 34, 286–297, 2012 (September)34, 286–297, 2012 (September) (September) 295 21. Cuervo AM, Palmer A, Rivett AJ, Knecht E. Degrada- tion of proteasomes by lysosomes in rat liver. Eur J Biochem 1995; 227: 792–800. 22. de Duve C. The lysosome. Sci Am 1963; 208: 64–72. 23. de Duve C, Wattiauz R. Function of lysosomes. Annu Rev Physiol 1966; 28: 435–92. 24. Degenhardt K, Mathew R, Beaudoin B, et al. Autophagy promotes tumor cell survival and restricts necrosis, inflamma- tion, and tumorigenesis. Cancer Cell 2006; 10: 51–64. 25. Dengjel J, Schoor O, Fischer R, et al. Autophagy pro- motes MHC class II presentation of peptides from intracellular source proteins. Proc Natl Acad Sci USA 2005; 102: 7922–7. 26. Dice JF. Chaperone-mediated autophagy. Autophagy 2007; 3: 295–9. 27. Dice JF, Chiang HL, Spencer EP, Backer JM. Regula- tion of catabolism of microinjected ribonuclease A. Identifi- cation of residues 7–11 as the essential pentapeptide. J Biol Chem 1986; 257: 14624–7. 28. Ding W-X, Ni H-M, Gao W, et al. Differential effects of endoplasmic reticulum stress-induced autophagy on sell survival. J Biol Chem 2007; 282: 4702–10. 29. Ding W-X, Ni H-M, Gao W, et al. Linking of autophagy to ubiquitin-proteasome system is important for the regulation of endoplasmic reticulum stress and cell viability. Am J Pathol 2007; 171: 513–24. 30. Dixon SJ, Lemberg KM, Lamprecht MR, et al. Fer- roptosis: an iron-dependent form of nonapoptotic cell death. Cell 2012; 149: 1060–72. 31. Djavaheri-Mergny M, Maiuri MC, Kroemer G. Cross talk between apoptosis and autophagy by caspase-mediated cleavage of Beclin 1. Oncogene 2010; 29: 1717–9. 32. Eskelinen E-L. Maturation of autophagic vacuoles in mammalian cells. Autophagy 2005; 1: 1–10. 33. Espina V, Mariani BD, Gallagher RI, et al. Malignant precursor cells pre-exist in human breast DCIS and require autophagy for survival. PLoS One 2010; 5: e10240. 34. Farré J-C, Subramani S. Peroxisome turnover by mi- cropexophagy: an autophagy-related process. Trends Cell Biol 2004; 14: 515–23. 35. Finn PF, Mesires NT, Vine M, Dice JF. Effects of small molecules on chaperone-mediated autophagy. Autophagy 2005; 1: 141–5. 36. Frankland-Searby S, Bhaumik SR. The 26S protea- some complex: an attractive target for cancer therapy. Biochim Biophys Acta 2012; 1825: 64–76. 37. Galluzzi L, Vitale I, Abrams JM, et al. Molecular definitions of cell death subroutines: recommendations of the Nomenclature Committee on Cell Death 2012. Cell Death Differ 2012; 19: 107–20. 38. Ganley IG, Lam du H, Wang J, et al. ULK1.ATG13.FIP200 com- plex mediates mTOR signaling and is essential for autophagy. J Biol Chem 2009; 284: 12297–305. 39. Garber K. Inducing indigestion: companies embrace autophagy inhibitors. J Natl Cancer Inst 2011; 9: 708–10. 40. Geetha T, Seibenhener ML, Chen L, et al. p62 serves as a shuttling factor for TrkA interaction with the proteasome. Biochem Biophys Res Commun 2008; 374: 33–7. 41. Hailey DW, Rambold AS, Satpute-Krishnan P, et al. Mitochondria supply membranes for autophagosome biogen- esis during starvation. Cell 2010; 141: 656–67. 42. Hayashi-Nishino M, Fujita N, Noda T, et al. A subdo- main of the endoplasmic reticulum forms a cradle for autopha- gosome formation. Nat Cell Biol 2009; 11: 1433–7. 43. Hetz C. The unfolded protein response: controlling cell fate decisions under ER stress and beyond. Nat Rev Mol Cell Biol 2012; 13: 89–102. 44. Hosokawa N, Hara T, Kaizuka T, et al. Nutrient-depen- dent mTORC1 association with the ULK1-Atg13-FIP200 com- plex required for autophagy. Mol Biol Cell 2009; 20: 1981–91. 45. Ichimura Y, Kirisako T, Takao T, et al. A ubiquitin-like system mediates protein lipidation. Nature 2000; 408: 488–92. 46. Inoki K, Kim J, Guan K-L. AMPK and mTOR in cellu- lar energy homeostasis and drug targets. Annu Rev Pharmacol Toxicol 2012; 52: 381–400. 47. Janku F, McConkey DJ, Hong DS, Kurzrock R. Au- tophagy as a target for anticancer therapy. Nat Rev Clin Oncol 2011; 8: 528–39. 48. Jiang J, Prasad K, Lafer EM, Sousa R. Structural basis of interdomain communication in the Hsc70 chaperone. Mol Cell 2005; 20: 513–24. 49. Jung CH, Jun CB, Ro S-H, et al. ULK-Atg13- FIP200 complexes mediate mTOR signaling to the autophagy machinery. Mol Biol Cell 2009; 20: 1992–2003. 50. Kanzawa T, Germano IM, Komata T, et al. Role of au- tophagy in temozolomide-induced cytotoxicity for malignant glioma cells. Cell Death Differ 2004; 11: 448–57. 51. Kaushik S, Massey AC, Mizushima N, Cuer- vo AM. Constitutive activation of chaperone-mediated autophagy in cells with impaired macroautophagy. Mol Biol Cell 2008; 19: 2179–92. 52. Kawaguchi T, Miyazawa K, Moriya S, et al. Combined treatment with bortezomib plus bafilomycin A1 enhances the cytocidal effect and induces endoplasmic reticulum stress in U266 myeloma cells: crosstalk among proteasome, autoph- agy-lysosome and ER stress. Int J Oncol 2011; 38: 643–54. 53. Kawaguchi Y, Kovacs JJ, McLaurin A, et al. The deacety- lase HDAC6 regulates aggresome formation and cell viability in response to misfolded protein stress. Cell 2003; 115: 727–38. 54. Kissová I, Salin B, Schaeffer J, et al. Selective and non-selective autophagic degradation of mitochondria in yeast. Autophagy 2007; 3: 329–36. 55. Kim D-S, Kim J-H, Lee G-H, et al. p38 Mitogen- activated protein kinase is involved in endoplasmic reticulum stress-induced cell death and autophagy in human gingival fibroblasts. Biol Pharm Bull 2010; 33: 545–9. 56. Kim E, Goraksha-Hicks P, Li L, et al. Regulation of TORC1 by Rag GTPases in nutrient response. Nat Cell Biol 2008; 10: 935–45. 57. Kim KW, Hwang M, Moretti L, et al. Autophagy upregulation by inhibitors of caspase-3 and mTOR enhances radiotherapy in a mouse model of lung cancer. Autophagy 2008; 4: 659–68. 58. Kim M-J, Woo S-J, Yoon C-H, et al. Involvement of autophagy in oncogenic K-Ras-induced malignant cell transformation. J Biol Chem 2011; 286: 12924–32. 59. Klionsky DJ. Autophagy revisited: A conversation with Christian de Duve. Autophagy 2008; 4: 740–3. 60. Klionsky DJ, Cregg JM, Dunn WA Jr, et al. A unified nomenclature for yeast autophagy-related genes. Dev Cell 2003; 5: 539–45. 61. Kon M, Kiffin R, Koga H, et al. Chaperone-mediated autophagy is required for tumor growth. Sci Transl Med 2012; 3: 109ra117. 62. Kong D, Ma S, Liang B, et al. The different regulatory effects of p53 status on multidrug resistance are determined by autophagy in ovarian cancer cells. Biomed Pharmacother 2012; 66: 271–8. 63. Korolchuk VI, Mansilla A, Menzies FM, Rubinsz- tein DC. Autophagy inhibition compromises degradation of ubiquitin-proteasome pathway substrates. Mol Cell 2009; 33: 517–27. 296 Experimental Oncology 34, 286–297, 2012 (September) 64. Korolchuk VI, Menzies FM, Rubinsztein DC. Mecha- nisms of cross-talk between the ubiquitin-proteasome and autophagy-lysosome systems. FEBS Lett 2010; 584: 1393–8. 65. Kouroku Y, Fujita E, Tanida I, et al. ER stress (PERK/ eIF2 alpha phosphorylation) mediates the polyglutamine- induced LC3 conversion, an essential step for autophagy formation. Cell Death Differ 2007; 14: 230–9. 66. Kremer JM. Rational use of new and existing disease- modifying agents in rheumatoid arthritis. Ann Intern Med 2001; 134: 695–706. 67. Krick R, Mühe Y, Prick T, et al. Piecemeal microau- tophagy of the nucleus: Genetic and morphological traits. Autophagy 2009; 5: 270–2. 68. Kroemer G, Galluzzi L, Vandenabeele P, et al. and Nomenclature Committee on Cell Death. Classification of cell death: recommendations of the Nomenclature Committee on Cell Death 2009. Cell Death Differ 2009; 16: 3–11. 69. Lazova R, Camp RL, Klump V, et al. Punctate LC3B expression is a common feature of solid tumors and associated with proliferation, metastasis, and poor outcome. Clin Cancer Res 2012; 18: 370–9. 70. Le X-F, Mao W, Lu Z, et al. Dasatinib induces au- tophagic cell death in human ovarian cancer. Cancer 2010; 116: 4980–90. 71. Lee AH, Chu GC, Iwakoshi NN, Glim cher LH. XBP-1 is re- quired for biogenesis of cellular secretory machinery of exocrine glands. EMBO J 2005; 24: 4368–80. 72. Lepine S, Allegood JC, Park M, et al. Sphingosine- 1-phosphate phosphohydrolase-1 regulates ER stress-induced autophagy. Cell Death Differ 2011; 18: 350–61. 73. Li H, Wang P, Sun Q, et al. Following cytochrome c release, autophagy is inhibited during chemotherapy-induced apoptosis by caspase 8-mediated cleavage of Beclin 1. Cancer Res 2011; 71: 3625–34. 74. Li J, Ni M, Lee B, et al. The unfolded protein response regulator GRP78/BiP is required for endoplasmic reticulum integrity and stress-induced autophagy in mammalian cells. Cell Death Differ 2008; 15: 1460–71. 75. Li WW, Li J, Bao JK. Microautophagy: lesser-known self-eating. Cell Mol Life Sci 2012; 69: 1125–36. 76. Li W, Yang Q, Mao Z. Chaperone-mediated auto- phagy: machinery, regulation and biological consequences. Cell Mol Life Sci 2011; 68: 749–63. 77. Li X, Ma Q, Wang J, et al. c-Abl and Arg tyrosine kinases regulate lysosomal degradation of the oncoprotein Galectin-3. Cell Death Differ 2010; 17: 1277–87. 78. Lin C-I, Whang EE, Abramson MA, et al. Autopha- gy: a new target for advanced papillary thyroid cancer therapy. Surgery 2009; 146: 1208–14. 79. Lindmo K, Stenmark H. Regulation of membrane traffic by phosphoinositide 3-kinases. J Cell Sci 2006; 119: 605–14. 80. Lu T-L, Huang G-J, Wang H-J, et al. Hispolon pro- motes MDM2 downregulation through chaperone-mediated autophagy. Biochem Biophys Res Commun 2010; 398: 26–31. 81. Lum JJ, DeBerardinis RJ, Thompson CB. Autophagy in metazoans: cell survival in the land of plenty. Nat Rev Mol Cell Biol 2005; 6: 439–48. 82. Müller O, Sattler T, Flötenmeyer M, et al. Autophagic tubes. The J Cell Biol 2000; 151: 519–28. 83. Massey AC, Kaushik S, Sovak G, et al. Consequences of the selective blockage of chaperone-mediated autophagy. Proc Natl Acad Sci USA 2006; 103: 5805–10. 84. Meusser B, Hirsch C, Jarosch E, Sommer T. ERAD: the long road to destruction. Nat Cell Biol 2005; 7: 766–72. 85. Milani M, Rzymski T, Mellor HR, et al. The role of ATF4 stabilization and autophagy in resistance of breast cancer cells treated with Bortezomib. Cancer Res 2009; 69: 4415–23. 86. Mizushima N, Yamamoto A, Hatano M, et al. Dissec- tion of autophagosome formation using Apg5-deficient mouse embryonic stem cells. J Cell Biol 2001; 152: 657–68. 87. Nishida Y, Arakawa S, Fujitani K, et al. Discovery of Atg5/Atg7-independent alternative macroautophagy. Na- ture 2009; 461: 654–8. 88. Noble CG, Dong J-M, Manser E, Song H. BclXL and UVRAG cause a monomer-dimer switch in Beclin1. J Biol Chem 2008; 283: 26274–82. 89. O’Neill PM, Bray PG, Hawley SR, et al. 4-Amino- quinolines — Past, present, and future: A chemical perspective. Pharmacol Ther 1998; 77: 29–58. 90. Ogata M, Hino S, Saito A, et al. Autophagy is activated for cell survival after endoplasmic reticulum stress. Mol Cell Biol 2006; 26: 9220–31. 91. Paglin S, Hollister T, Delohery T, et al. A novel response of cancer cells to radiation involves autophagy and formation of acidic vesicles. Cancer Res 2001; 61: 439–44. 92. Pan Y, Gao Y, Chen L, et al. Targeting autophagy augments in vitro and in vivo antimyeloma activity of DNA- damaging chemotherapy. Clin Cancer Res 2011; 17: 3248–58. 93. Parmar VM, Schroder M. Sensing endoplasmic reticu- lum stress. Adv Exp Med Biol 2012; 738: 153–68. 94. Pattingre S, Tassa A, Qu X, et al. Bcl-2 antiapoptotic proteins inhibit Beclin 1-dependent autophagy. Cell 2005; 122: 927–39. 95. Petiot A, Ogier-Denis E, Blommaart EF, et al. Distinct classes of phosphatidylinositol 3’-kinases are involved in sig- naling pathways that control macroautophagy in HT-29 cells. J Biol Chem 2000; 275: 992–8. 96. Pickart CM. Mechanisms underlying ubiquitination. Ann Rev Biochem 2001; 70: 503–33. 97. Polson HE, de Lartigue J, Rigden DJ, et al. Mammalian Atg18 (WIPI2) localizes to omegasome-anchored phago phores and positively regulates LC3 lipidation. Autophagy 2010; 6: 506–22. 98. Popovic D, Dikic I. The molecular basis of selective autophagy. Biochemist 2012; 34: 24–30. 99. Ravikumar B, Acevedo-Arozena A, Imarisio S, et al. Dynein mutations impair autophagic clearance of aggregate- prone proteins. Nat Genet 2005; 37: 771–6. 100. Ravikumar B, Moreau K, Jahreiss L, et al. Plasma membrane contributes to the formation of pre-autophago- somal structures. Nat Cell Biol 2010; 12: 747–57. 101. Rez G, Csak J, Fellinger E, et al. Time course of vinblas- tine-induced autophagocytosis and changes in the endoplasmic reticulum in murine pancreatic acinar cells: a morphometric and biochemical study. Eur J Cell Biol 1996; 71: 341–50. 102. Romanelli F, Smith KM, Hoven AD. Chloroquine and hydroxychloroquine as inhibitors of human immunodeficiency virus (HIV-1) activity Curr Pharm Des 2004; 10: 2643–8. 103. Rovetta F, Stacchiotti A, Consiglio A, et al. ER sig- naling regulation drives the switch between autophagy and apoptosis in NRK-52E cells exposed to cisplatin. Exp Cell Res 2012; 318: 238–50. 104. Rutkowski DT, Arnold SM, Miller CN, et al. Adapta- tion to ER stress is mediated by differential stabilities of pro- survival and pro-apoptotic mRNAs and proteins. PLoS Biol 2006; 4: e374. 105. Sancak Y, Peterson TR, Shaul YD, et al. The Rag GTPases bind Raptor and mediate amino acid signaling to mTORC1. Science 2008; 320: 1496–501. 106. Sattler T, Mayer A. Cell-free reconstitution of micro- autophagic vacuole invagination and vesicle formation. J Cell Biol 2000; 151: 529–38. Experimental Oncology 34, 286–297, 2012 (September)34, 286–297, 2012 (September) (September) 297 107. Shen S, Kepp O, Michaud M, et al. Association and dissociation of autophagy, apoptosis and necrosis by systematic chemical study. Oncogene 2011; 30: 4544–56. 108. Shimizu S, Konishi A, Nishida Y, et al. Involvement of JNK in the regulation of autophagic cell death. Oncogene 2010; 29: 2070–82. 109. Sotelo J, Briceño E, López-González MA. Adding chloroquine to conventional treatment for glioblastoma mul- tiforme. Ann Intern Med 2006; 144: 337–43. 110. Tallóczy Z, Jiang W, Virgin HW 4th, et al. Regulation of starvation- and virus-induced autophagy by the eIF2alpha kinase signaling pathway. Proc Natl Acad Sci USA 2002; 99: 190–5. 111. Tang D, Kang R, Livesey KM, et al. Endogenous HMGB1 regulates autophagy. J Cell Biol 2010; 190: 881–92. 112. Tanida I. Autophagy basics. Microbiol Immunol 2011; 55: 1–11. 113. Vance JE, Vance DE. Phospholipid biosynthesis in mammalian cells. Biochem Cell Biol 2004; 82: 113–28. 114. Venugopal B, Mesires NT, Kennedy JC, et al. Chape- rone-mediated autophagy is defective in mucolipidosis type IV. J Cell Physiol 2009; 219: 344–53. 115. Wang Y, Singh R, Massey AC, et al. Loss of macroau- tophagy promotes or prevents fibroblast apoptosis depending on the death stimulus. J Biol Chem 2008; 283: 4766–77. 116. Wei Y, Pattingre S, Sinha S, et al. JNK1-mediated phosphorylation of Bcl-2 regulates starvation-induced au- tophagy. Mol Cell 2008; 30: 678–88. 117. Wei Y, Sinha S, Levine B. Dual role of JNK1-mediated phosphorylation of Bcl-2 in autophagy and apoptosis regula- tion. Autophagy 2008; 4: 949–51. 118. Weinstein IB, Joe A. Oncogene addiction. Cancer Res 2008; 68: 3077–80. 119. Welchman RL, Gordon C, Mayer RJ. Ubiquitin and ubiquitin-like proteins as multifunctional signals. Nat Rev Mol Cell Biol 2005; 6: 599–609. 120. Wirawan E, Vande Walle L, Kersse K, et al. Caspase-me- diated cleavage of Beclin-1 inactivates Beclin-1-induced autophagy and enhances apoptosis by promoting the release of proapoptotic factors from mitochondria. Cell Death Dis 2010; 1: e18. 121. Wooten MW, Geetha T, Babu JR, et al. Essential role of sequestosome 1/p62 in regulating accumulation of Lys63- ubiquitinated proteins. J Biol Chem 2008; 283: 6783–9. 122. Yamamoto A, Tagawa Y, Yoshimori T, et al. Bafilomycin A1 prevents maturation of autophagic vacuoles by inhibiting fu- sion between autophagosomes and lysosomes in rat hepatoma cell line, H-4-II-E cells. Cell Struct Funct 1998; 23: 33–42. 123. Yang Z, Klionsky DJ. Mammalian autophagy: core molecular machinery and signaling regulation. Curr Opin Cell Biol 2011; 22: 124–31. 124. Yao KC, Komata T, Kondo Y, et al. Molecular response of human glioblastoma multiforme cells to ionizing radia- tion: cell cycle arrest, modulation of the expression of cyclin- dependent kinase inhibitors, and autophagy. J Neurosurg 2003; 98: 378–84. 125. Ye Y, Shibata Y, Kikkert M, et al. Recruitment of the p97 ATPase and ubiquitin ligases to the site of retrotransloca- tion at the endoplasmic reticulum membrane. Proc Natl Acad Sci USA 2005; 102: 14132–8. 126. Yoon YH, Cho KS, Hwang JJ, et al. Induction of lysosomal dilatation, arrested autophagy, and cell death by chloroquine in cultured ARPE-19 cells. Invest Ophthalmol Vis Sci 2010; 51: 6030–7. 127. Yousefi S, Perozzo R, Schmid I, et al. Calpain- mediated cleavage of Atg5 switches autophagy to apoptosis. Nat Cell Biol 2006; 8: 1124–32. 128. Zhang N, Qi Y, Wadham C, et al. FTY720 induces necrotic cell death and autophagy in ovarian cancer cells: a pro- tective role of autophagy. Autophagy 2010; 6: 1157–67. 129. Zhu K, Dunner K Jr, McConkey DJ. Proteasome inhibitors activate autophagy as a cytoprotective response in human prostate cancer cells. Oncogene 2010; 29: 451–62. Copyright © Experimental Oncology, 2012