Comparative analysis of epigenetic markers in plasma and tissue of patients with colorectal cancer

Aim. The work is devoted to the development of less invasive tools for the colorectal cancer (CRC) screening. Methods. Q-PCR and methylation-specific PCR techniques were used in the current work. Results. We have shown that the levels of cell-free plasma DNA are higher in the CRC patients compared w...

Full description

Saved in:
Bibliographic Details
Published in:Вiopolymers and Cell
Date:2014
Main Authors: Kondratov, A.G., Nekrasov, K.A., Lototska, L.V., Panasenko, G.V., Stoliar, L.A., Lapska, Y.V., Kolesnyk, O.O., Shchepotin, I.B., Rynditch, A.V., Kashuba, V.I.
Format: Article
Language:English
Published: Інститут молекулярної біології і генетики НАН України 2014
Subjects:
Online Access:https://nasplib.isofts.kiev.ua/handle/123456789/153751
Tags: Add Tag
No Tags, Be the first to tag this record!
Journal Title:Digital Library of Periodicals of National Academy of Sciences of Ukraine
Cite this:Comparative analysis of epigenetic markers in plasma and tissue of patients with colorectal cancer / A.G. Kondratov, K.A. Nekrasov, L.V. Lototska, G.V. Panasenko, L.A. Stoliar, Y.V. Lapska, O.O. Kolesnyk, I.B. Shchepotin, A.V. Rynditch, V.I. Kashuba // Вiopolymers and Cell. — 2014. — Т. 30, № 2. — С. 129-134. — Бібліогр.: 19 назв. — англ.

Institution

Digital Library of Periodicals of National Academy of Sciences of Ukraine
id nasplib_isofts_kiev_ua-123456789-153751
record_format dspace
spelling Kondratov, A.G.
Nekrasov, K.A.
Lototska, L.V.
Panasenko, G.V.
Stoliar, L.A.
Lapska, Y.V.
Kolesnyk, O.O.
Shchepotin, I.B.
Rynditch, A.V.
Kashuba, V.I.
2019-06-14T15:09:33Z
2019-06-14T15:09:33Z
2014
Comparative analysis of epigenetic markers in plasma and tissue of patients with colorectal cancer / A.G. Kondratov, K.A. Nekrasov, L.V. Lototska, G.V. Panasenko, L.A. Stoliar, Y.V. Lapska, O.O. Kolesnyk, I.B. Shchepotin, A.V. Rynditch, V.I. Kashuba // Вiopolymers and Cell. — 2014. — Т. 30, № 2. — С. 129-134. — Бібліогр.: 19 назв. — англ.
0233-7657
DOI: http://dx.doi.org/10.7124/bc.00088B
https://nasplib.isofts.kiev.ua/handle/123456789/153751
577.218 + 577.133.4
Aim. The work is devoted to the development of less invasive tools for the colorectal cancer (CRC) screening. Methods. Q-PCR and methylation-specific PCR techniques were used in the current work. Results. We have shown that the levels of cell-free plasma DNA are higher in the CRC patients compared with the healthy donors (p < 0.01). Hypermethylation of APC, FHIT, LRRC3B and HIC1 genes was studied in the tumor and plasma samples of CRC patients. Two-stage verification for CRC screening was proposed. Conclusions. We proposed and tested a novel approach for CRC screening based on the determination of cell-free DNA and methylated DNA fragments in the plasma.
Мета. Розробка менш інвазивних методик для скринінгу злоякісних пухлин товстого кишечника (CRC). Методи. Використано кількісну ПЛР і метил-специфічну ПЛР. Результати. Показано, що середнє значення концентрацій вільно циркулюючої ДНК у плазмі крові є статистично достовірно вищим у пацієнтів з CRC порівняно зі здоровими донорами (p < 0,01). Встановлено гіперметилювання генів APC, FHIT, LRRC3B і HIC1 у пухлинах та плазмі хворих на CRC. Висновки. Нами запропоновано і перевірено новітній підхід для скринінгу CRC, який базується на визначенні позаклітинної ДНК і метильованих фрагментів ДНК у плазмі.
Цель. Разработка менее инвазивных методик для скрининга злокачественных опухолей толстого кишечника (CRC). Методы. Использована количественная ПЦР и метил-специфическая ПЦР. Результаты. Показано, что среднее значение свободно циркулирующей ДНК в плазме статистически достоверно выше у пациентов с CRC по сравнению со здоровыми донорами (p < 0,01). Установлено гиперметилирование генов APC, FHIT, LRRC3B и HIC1 в опухолях и плазме пациентов с CRC. Выводы. Нами предложен и проверен новейший подход для скрининга CRC, базирующийся на определении внеклеточной ДНК и метилированных фрагментов ДНК в плазме.
en
Інститут молекулярної біології і генетики НАН України
Вiopolymers and Cell
Biomedicine
Comparative analysis of epigenetic markers in plasma and tissue of patients with colorectal cancer
Порівняльний аналіз епігенетичних маркерів у плазмі крові пацієнтів, хворих на рак товстого кишечника
Сравнительный анализ эпигенетических маркеров в плазме крови пациентов, больных раком толстого кишечника
Article
published earlier
institution Digital Library of Periodicals of National Academy of Sciences of Ukraine
collection DSpace DC
title Comparative analysis of epigenetic markers in plasma and tissue of patients with colorectal cancer
spellingShingle Comparative analysis of epigenetic markers in plasma and tissue of patients with colorectal cancer
Kondratov, A.G.
Nekrasov, K.A.
Lototska, L.V.
Panasenko, G.V.
Stoliar, L.A.
Lapska, Y.V.
Kolesnyk, O.O.
Shchepotin, I.B.
Rynditch, A.V.
Kashuba, V.I.
Biomedicine
title_short Comparative analysis of epigenetic markers in plasma and tissue of patients with colorectal cancer
title_full Comparative analysis of epigenetic markers in plasma and tissue of patients with colorectal cancer
title_fullStr Comparative analysis of epigenetic markers in plasma and tissue of patients with colorectal cancer
title_full_unstemmed Comparative analysis of epigenetic markers in plasma and tissue of patients with colorectal cancer
title_sort comparative analysis of epigenetic markers in plasma and tissue of patients with colorectal cancer
author Kondratov, A.G.
Nekrasov, K.A.
Lototska, L.V.
Panasenko, G.V.
Stoliar, L.A.
Lapska, Y.V.
Kolesnyk, O.O.
Shchepotin, I.B.
Rynditch, A.V.
Kashuba, V.I.
author_facet Kondratov, A.G.
Nekrasov, K.A.
Lototska, L.V.
Panasenko, G.V.
Stoliar, L.A.
Lapska, Y.V.
Kolesnyk, O.O.
Shchepotin, I.B.
Rynditch, A.V.
Kashuba, V.I.
topic Biomedicine
topic_facet Biomedicine
publishDate 2014
language English
container_title Вiopolymers and Cell
publisher Інститут молекулярної біології і генетики НАН України
format Article
title_alt Порівняльний аналіз епігенетичних маркерів у плазмі крові пацієнтів, хворих на рак товстого кишечника
Сравнительный анализ эпигенетических маркеров в плазме крови пациентов, больных раком толстого кишечника
description Aim. The work is devoted to the development of less invasive tools for the colorectal cancer (CRC) screening. Methods. Q-PCR and methylation-specific PCR techniques were used in the current work. Results. We have shown that the levels of cell-free plasma DNA are higher in the CRC patients compared with the healthy donors (p < 0.01). Hypermethylation of APC, FHIT, LRRC3B and HIC1 genes was studied in the tumor and plasma samples of CRC patients. Two-stage verification for CRC screening was proposed. Conclusions. We proposed and tested a novel approach for CRC screening based on the determination of cell-free DNA and methylated DNA fragments in the plasma. Мета. Розробка менш інвазивних методик для скринінгу злоякісних пухлин товстого кишечника (CRC). Методи. Використано кількісну ПЛР і метил-специфічну ПЛР. Результати. Показано, що середнє значення концентрацій вільно циркулюючої ДНК у плазмі крові є статистично достовірно вищим у пацієнтів з CRC порівняно зі здоровими донорами (p < 0,01). Встановлено гіперметилювання генів APC, FHIT, LRRC3B і HIC1 у пухлинах та плазмі хворих на CRC. Висновки. Нами запропоновано і перевірено новітній підхід для скринінгу CRC, який базується на визначенні позаклітинної ДНК і метильованих фрагментів ДНК у плазмі. Цель. Разработка менее инвазивных методик для скрининга злокачественных опухолей толстого кишечника (CRC). Методы. Использована количественная ПЦР и метил-специфическая ПЦР. Результаты. Показано, что среднее значение свободно циркулирующей ДНК в плазме статистически достоверно выше у пациентов с CRC по сравнению со здоровыми донорами (p < 0,01). Установлено гиперметилирование генов APC, FHIT, LRRC3B и HIC1 в опухолях и плазме пациентов с CRC. Выводы. Нами предложен и проверен новейший подход для скрининга CRC, базирующийся на определении внеклеточной ДНК и метилированных фрагментов ДНК в плазме.
issn 0233-7657
url https://nasplib.isofts.kiev.ua/handle/123456789/153751
citation_txt Comparative analysis of epigenetic markers in plasma and tissue of patients with colorectal cancer / A.G. Kondratov, K.A. Nekrasov, L.V. Lototska, G.V. Panasenko, L.A. Stoliar, Y.V. Lapska, O.O. Kolesnyk, I.B. Shchepotin, A.V. Rynditch, V.I. Kashuba // Вiopolymers and Cell. — 2014. — Т. 30, № 2. — С. 129-134. — Бібліогр.: 19 назв. — англ.
work_keys_str_mv AT kondratovag comparativeanalysisofepigeneticmarkersinplasmaandtissueofpatientswithcolorectalcancer
AT nekrasovka comparativeanalysisofepigeneticmarkersinplasmaandtissueofpatientswithcolorectalcancer
AT lototskalv comparativeanalysisofepigeneticmarkersinplasmaandtissueofpatientswithcolorectalcancer
AT panasenkogv comparativeanalysisofepigeneticmarkersinplasmaandtissueofpatientswithcolorectalcancer
AT stoliarla comparativeanalysisofepigeneticmarkersinplasmaandtissueofpatientswithcolorectalcancer
AT lapskayv comparativeanalysisofepigeneticmarkersinplasmaandtissueofpatientswithcolorectalcancer
AT kolesnykoo comparativeanalysisofepigeneticmarkersinplasmaandtissueofpatientswithcolorectalcancer
AT shchepotinib comparativeanalysisofepigeneticmarkersinplasmaandtissueofpatientswithcolorectalcancer
AT rynditchav comparativeanalysisofepigeneticmarkersinplasmaandtissueofpatientswithcolorectalcancer
AT kashubavi comparativeanalysisofepigeneticmarkersinplasmaandtissueofpatientswithcolorectalcancer
AT kondratovag porívnâlʹniianalízepígenetičnihmarkerívuplazmíkrovípacíêntívhvorihnaraktovstogokišečnika
AT nekrasovka porívnâlʹniianalízepígenetičnihmarkerívuplazmíkrovípacíêntívhvorihnaraktovstogokišečnika
AT lototskalv porívnâlʹniianalízepígenetičnihmarkerívuplazmíkrovípacíêntívhvorihnaraktovstogokišečnika
AT panasenkogv porívnâlʹniianalízepígenetičnihmarkerívuplazmíkrovípacíêntívhvorihnaraktovstogokišečnika
AT stoliarla porívnâlʹniianalízepígenetičnihmarkerívuplazmíkrovípacíêntívhvorihnaraktovstogokišečnika
AT lapskayv porívnâlʹniianalízepígenetičnihmarkerívuplazmíkrovípacíêntívhvorihnaraktovstogokišečnika
AT kolesnykoo porívnâlʹniianalízepígenetičnihmarkerívuplazmíkrovípacíêntívhvorihnaraktovstogokišečnika
AT shchepotinib porívnâlʹniianalízepígenetičnihmarkerívuplazmíkrovípacíêntívhvorihnaraktovstogokišečnika
AT rynditchav porívnâlʹniianalízepígenetičnihmarkerívuplazmíkrovípacíêntívhvorihnaraktovstogokišečnika
AT kashubavi porívnâlʹniianalízepígenetičnihmarkerívuplazmíkrovípacíêntívhvorihnaraktovstogokišečnika
AT kondratovag sravnitelʹnyianalizépigenetičeskihmarkerovvplazmekrovipacientovbolʹnyhrakomtolstogokišečnika
AT nekrasovka sravnitelʹnyianalizépigenetičeskihmarkerovvplazmekrovipacientovbolʹnyhrakomtolstogokišečnika
AT lototskalv sravnitelʹnyianalizépigenetičeskihmarkerovvplazmekrovipacientovbolʹnyhrakomtolstogokišečnika
AT panasenkogv sravnitelʹnyianalizépigenetičeskihmarkerovvplazmekrovipacientovbolʹnyhrakomtolstogokišečnika
AT stoliarla sravnitelʹnyianalizépigenetičeskihmarkerovvplazmekrovipacientovbolʹnyhrakomtolstogokišečnika
AT lapskayv sravnitelʹnyianalizépigenetičeskihmarkerovvplazmekrovipacientovbolʹnyhrakomtolstogokišečnika
AT kolesnykoo sravnitelʹnyianalizépigenetičeskihmarkerovvplazmekrovipacientovbolʹnyhrakomtolstogokišečnika
AT shchepotinib sravnitelʹnyianalizépigenetičeskihmarkerovvplazmekrovipacientovbolʹnyhrakomtolstogokišečnika
AT rynditchav sravnitelʹnyianalizépigenetičeskihmarkerovvplazmekrovipacientovbolʹnyhrakomtolstogokišečnika
AT kashubavi sravnitelʹnyianalizépigenetičeskihmarkerovvplazmekrovipacientovbolʹnyhrakomtolstogokišečnika
first_indexed 2025-11-24T04:42:08Z
last_indexed 2025-11-24T04:42:08Z
_version_ 1850841707595169792
fulltext BIOMEDICINE UDC 577.218 + 577.133.4 Comparative analysis of epigenetic markers in plasma and tissue of patients with colorectal cancer A. G. Kondratov1, K. A. Nekrasov1, L. V. Lototska1, G. V. Panasenko1, L. A. Stoliar1, Y. V. Lapska1, O. O. Kolesnyk2, I. B. Shchepotin2, A. V. Rynditch1, V. I. Kashuba1, 3 1State Key Laboratory of Molecular and Cellular Biology, Institute of Molecular Biology and Genetics, NAS of Ukraine 150, Akademika Zabolotnoho Str., Kyiv, Ukraine, 03680 2National Cancer Institute 33/43, Lomonosova Str., Kyiv, Ukraine, 03022 3Department of Microbiology, Tumor and Cell Biology, Karolinska Institutet Nobels vag 16, Box 280, 171 77-Stockholm, o.g.kondratov@imbg.org.ua Aim. The work is devoted to the development of less invasive tools for the colorectal cancer (CRC) screening. Methods. Q-PCR and methylation-specific PCR techniques were used in the current work. Results. We have shown that the levels of cell-free plasma DNA are higher in the CRC patients compared with the healthy donors (p < 0.01). Hypermethylation of APC, FHIT, LRRC3B and HIC1 genes was studied in the tumor and plasma samples of CRC patients. Two-stage verification for CRC screening was proposed. Conclusions. We proposed and tested a novel approach for CRC screening based on the determination of cell-free DNA and methylated DNA fragments in the plasma. Keywords: colorectal cancer, cell-free DNA, DNA methylation, APC, FHIT, LRRC3B, HIC1. Introduction. Colorectal cancer (CRC) is the third com- monly diagnosed cancer that causes more than 600 000 deaths per year worldwide [1]. In most cases, CRC tu- mors grow slowly – approximately 1 cm per year with- out noticeable symptoms. The most sensitive modern diagnostic tool for the CRC detection is a colonoscopy. It allows detecting the tumors of less than 1 cm. How- ever, the colonoscopy procedure is painful and in some cases is not recommended to the patients with heart di- seases, because of possible adverse cardiopulmonary re- actions that are usually related to the sedation [2] as the colonoscopy is performed under narcosis. Also, the co- lonoscopy meets some difficulties in case of altered to- pography of a colon [3]. Thus, the development of less invasive tools for screening CRC is a relevant problem of the modern oncology. DNA methylation is a stable epigenetic mark which is associated with gene silencing in the case of promo- ter localization in CpG-island [4]. The gene hyperme- thylation frequently targets the potential tumor-sup- pressor genes (TSG), inactivation of which promotes the tumor development. According to Toyota et al., the colon cancer can be ascribed to the tumors with a high frequency of gene hypermethylation. Approximately 17 % of CpG-islands are hypermethylated in CRC [5]. The circulating cancer cells and cell-free DNA (cf DNA) are frequently detected in the patients with diffe- rent types of the malignant disease. Moreover, a level of cfDNA is elevated in the cancer patients in compa- rison with the healthy individuals [6]. In the proposed paper DNA hypermethylation of the well-known tumor associated genes like LRRC3B, FHIT, APC and HIC1 was detected by methylation- specific PCR (MSP) in the plasma and tumor samples 129 ISSN 0233–7657. Biopolymers and Cell. 2014. Vol. 30. N 2. P. 129–134 doi: http://dx.doi.org/10.7124/bc.00088B � Institute of Molecular Biology and Genetics, NAS of Ukraine, 2014 from the CRC patients [7–10]. Adjacent to the tumor non-malignant tissues of bowel were used as a control. Additionally, the levels of cfDNA in plasma from the CRC patients and healthy donors were mesuared by quantitative PCR (Q-PCR). All experiments were car- ried out with the tumors, adjacent non-malignant tis- sues and plasma samples of the same patients. Material and methods. Ethics statements. The samp- les were collected in accordance with the Declaration of Helsinki and approved by the guidelines issued by the Ethic Committee of the National Cancer Institute of the Academy of Medical Sciences, Kyiv, Ukraine. Sample collection, genomic and cell-free DNA iso- lation. Twenty surgically excised tissue samples of CRC were used in the present study (Table 1). All tumor samples were paired with non-malignant tissues, which were taken as the normal tissue samples. Immediately after surgery, the tissue samples were frozen in liquid nitrogen and stored at –70 oC. Neither chemotherapy nor radiotherapy was conducted for any patients prior to surgery. Each tissue sample was accompanied by a cor- responding blood sample. All tissue samples were cha- racterized histologically. Blood of 21 healthy donors was used as a control group. Genomic DNA was purified by GenElute Mamma- lian Genomic DNA Miniprep Kit («Sigma-Aldrich», USA) according to the manufacturer’s recommen- dations. Briefly, 50 mg of tissue were homogenized in liquid nitrogen, subjected to lysis and purified with GenElute Miniprep Binding Columns. The quality and size of genomic DNA were assessed by gel electro- phoresis («Sigma-Aldrich»). Plasma from the cancer patients and the healthy donors was obtained by the multistage centrifugation of the blood in range from 1000 to 3000 g, using EDTA as an anticoagulant. The cell free circulating DNA from 200 �l of plasma was isolated by the Proba NK DNA («DNA Technology», Russia) isolation kit, according to the manufacturer’s instructions. Determination of concentrations of cell free DNA. To detect the concentration of cell free circulating DNA in the plasma, the Q-PCR was used. The Q-PCR was performed with SYBR Green mixture («Thermo Scientific», USA) and primers for the GAPDH gene: gRef For 5'-GGCTCCCACCTTTCTCATC-3' and gRef Rev 5'-AGCGTACTCCCCACATCA-3', using the following reaction conditions: 95 oC – 4 min, then 35 cycles at 95 oC – 15 s, 60 oC – 20 s and 72 oC – 30 s. To carry out Q-PCR the CFX real-time PCR detection system («BioRad», USA) was used. To determine the concentration of DNA in the plasma the calibration cur- ve in coordinates of genomic DNA concentrations and Ct was plotted. The range of genomic DNA concent- ration was 2.44–2440 pg. The range of concentrations was created by DNA dilution. The initial concentration of DNA for a calibration curve was determined by means of ND-2000 («Thermo Scientific»). DNA bisulfite conversion and determination of me- thylated DNA fragments. The bisulfite treatment of ge- 130 KONDRATOV A. G. ET AL. N, CRC patients cfDNA concentration for CRC patients, ng/ml N, healthy donors cfDNA concentration for healthy donors, ng/ml 100 14.0 1 6.1 102 4.5 2 7.8 103 8.6 3 5.3 104 7.1 4 7.9 108 10.3 5 10.0 109 11.9 6 5.4 110 25.5 7 6.8 116 3.2 8 11.0 117 2.7 9 5.3 118 12.6 10 6.7 119 10.7 11 2.7 120 23.8 12 3.2 121 12.1 13 6.3 122 69.9 14 4.8 124 15.1 15 3.9 126 18.2 16 6.0 127 21.1 17 18.8 129 36.5 18 8.2 130 10.8 19 8.3 131 32.8 – – 132 252.7 – – Table 1 Concentrations of cfDNA in plasma samples of CRC patients and healthy donors nomic DNA was performed, using the EZ DNA Me- thylation kit («ZYMO Research», USA), according to the manufacturer’s protocol. For the bisulfite treatment of the plasma DNA 44 �l of solution of the dissolved DNA sediments with co-precipitator were used. To pro- tect the plasma DNA during the reaction, 450 ng of Lam- bda DNA were added per a reaction sample of bisulfite treatment.The bisulfite treated DNA was dissolved in 20 �l of Elution buffer. To determine the methylation status of the LRRC3B, APC, FHIT, and HIC1 genes in tissue samples, the me- thylation-specific PCR (MSP) was used. MSP was per- formed using primers that were described previously [11–14]. Amplification of the bisulfite converted sequ- ence of the COL2A1 gene was used as a control of the DNA input [14]. The PCR mixture of MSP reactions contained 10 � PCR Dream buffer («Thermo Scien- tific»), 0.2 mM deoxyribonucleotide triphosphates (dNTPs), 0.3 µM primers, 50 ng of modified DNA and 1 U of DreamTaq polymerase («Thermo Scientific»). Amplification was performed for 40 cycles (30 s at 95 oC, 30 s at 63 oCand 30 s at 72 oC), initiated with DNA denaturation at 95 oC for 4 min. The final exten- sion was at 72 oC for 5 min. Amplified products were detected by electrophoresis in 12 % polyacrylamide gel with subsequent ethidium bromide staining. To determine methylation status of the APC, FHIT, LRRC3B, and HIC1 genes in the cell free circulating DNA, the real-time MSP (RT-MSP) was used. RT- MSP was performed with the above-mentioned primer set for MSP. Each sample of the amplification reaction contained 1 � SYBR Green mixture («Thermo Scien- tific»), 0.4 µM of each primer and 4�l of bisulfite trea- ted DNA. The conditions of RT-MSP were 95 oC for 10 min, for 50 cycles; 95 oC for 15 s, 62–65 oC for 20 s and 72 oC for 30 s. It was considered the positive methy- lation status of the sample if Ct of reaction was < 45 cycles. The quality of amplified products was checked by electrophoresis in 2.5 % agarose gel and melting curve analysis with the CFX real-time PCR detection system («BioRad»). To verify RT-MSP data, the MSP sequencing assay was performed. Statistical analysis. Statistical analysis was perfor- med using STATISTICA 7.0 program («StatSoft Inc», USA). If the p-value was < 0.05 the results were consi- dered statistically significant. The nonparametric Mann- Whitney U Test was used to calculate the difference bet- ween concentration of plasma cfDNA in CRC patients and healthy donors. Results and discussion. The levels of cell free cir- culating DNA in the plasma from CRC patients are hi- gher than in healthy donors. Using Q-PCR, the level of cell free circulating DNA was determined in the plasma of CRC patients and healthy donors (Table 1, Figure). It was shown that the mean value of concentration of plasma cfDNA was significantly higher in CRC pati- ents, compared with the healthy donors (p < 0.01). Thus, the mean value (MV) of concentration of cell-free cir- culating DNA in the plasma from CRC patients was 29.45 ± 12.24 ng/ml (MV ± St. Error), whereas it was 7.07 ± 0.82 (MV ± St. Error) in healthy donors. In order to generate the upper cut-off value of the cell free circu- lating DNA concentration in plasma we used the highest permissible concentration in the healthy donors. It was defined as a mean value concentration of cfDNA of healthy donors and three standard deviations. So, the upper cut-off value of the free-circulating DNA concent- ration was 17.7 ng/ml of the plasma in healthy donors (Figure). Therefore, there were 8 out of 20 samples of CRC which fell into criteria as samples with an abnormally increased DNA level. Hypermethylation of tumor suppressor genes in the cancer tissues and plasma samples from CRC patients. APC, FHIT, LRRC3B and HIC1 are the colon cancer as- 131 COMPARATIVE ANALYSIS OF EPIGENETIC MARKERS OF PATIENTS WITH COLORECTAL CANCER cf D N A co nc en tr at io n , ng /m L 1 2 0 10 20 30 40 50 60 70 CfDNA concentration in plasma of 20 CRC patients (1) and 19 healthy donors (2) was detected by Q-PCR. The upper cut-off value of the free-circulating DNA concentration of healthy donors is depicted as a dashed line at 17.7 ng/ml level of plasma. To prevent merger of data points one CRC (N 132) concentration was not included here, it equals 252,7 ng/ml sociated genes. Their alterations due to the promoter CpG-island methylation were described previously. Thus, hypermethylation of APC, FHIT, LRRC3B and HIC1 was detected in 45, 37, 77 and 42 % of CRC samples correspondingly [15–18]. Therefore, the MSP- based detection of the methylated fragments of these ge- nes was used for further development of screening pa- nel for CRC. In the current research we have found that the APC, FHIT, and LRRC3B genes were hypermethy- lated in 50 % (10/20), 70 % (14/20) and 65 % (13/20) of tumor samples, correspondingly. Altogether, the hyper- methylation of at least one of the selected genes was de- tected in 90 % (18/20) of samples. Using MSP and the subsequent melting curve ana- lysis, the methylated fragments of APC, FHIT and LRRC3B genes were detected in 30 % (6/20), 20 % (4/20) and 15 % (3/20) of the plasma of CRC patients, respectively. The hypermethylation of at least one se- lected gene was found in 50 % (10/20) of the plasma samples from CRC patients. 132 KONDRATOV A. G. ET AL. Tissue Plasma N/Genes LRRC3B APC FHIT Totally LRRC3B APC FHIT cfDNA Totally 100 M M M + ND M ND L A 102 U M U + ND M ND L A 103 U U U – ND ND ND L NC 104 M U M + M ND ND L A 108 M U U + ND ND ND L NC 109 M U U + ND ND ND L NC 110 M M M + ND ND M H A 116 M M U + ND ND ND L NC 117 M M M + ND ND ND L NC 118 M M M + ND M ND L A 119 U M M + ND M M L A 120 U U M + ND ND ND H A 121 M U M + ND ND M L A 122 M M M + ND ND ND H A 126 U U M + ND ND ND H A 127 M M M + ND ND ND H A 129 M U M + M ND M H A 130 U U U – ND M ND L A 131 U U M + ND ND ND H A 132 M M M + M M ND H A Frequency 65 % (13/20) 50 % (10/20) 70 % (14/20) 90 % (18/20) 15 % (3/20) 30 % (6/20) 20 % (4/20) 40 % (8/20) 75 % (15/20) N o t e . M – methylated DNA was detected; U – unmethylated DNA was detected; H – cfDNA concentration is higher than upper cut-off value; L – cfDNA concentration is lower than upper cut-off value; ND – methylated DNA was not detected; «+» – methylation was detected in one or more genes for the tissue; «–» – no methylation was detected for at least one genes for the tissue; A – abnormal plasma; NC – no changes have been de- tected in the plasma. Table 2 Total data of cfDNA concentration and methylation of APC, FHIT and LRRC3B genes from plasma of CRC patients. No amplification was found in reactions with MSP primers and bisulfite treated Lambda DNA which did not include the human DNA. No methylated fragments of the selected genes were identified in plasma of heal- thy donors. Therefore, the hypermethylated fragments of APC, FHIT, and LRRC3B genes in the plasma were detected in 50 % (5/10), 31 % (4/13) and 23 % (3/13) of tumors which were positive for hypermethylated fragments of the abovementioned genes, respectively. To verify speci- ficity of MSP, the PCR products of the APC and LRRC3B genes were sequenced after amplification with the pri- mers for methylated DNA. To study specificity of the gene panel, hypermethy- lation of the APC, FHIT and LRRC3B genes was stu- died in the plasma of healthy donors. Moreover, the me- thylation of APC, FHIT and LRRC3B in plasma was de- tected in 92 % (12/13) of the samples with pre-detected methylation of these genes in tumor tissue. Initially we had shown the same tendency in hypermethylation of the APC, FHIT and LRRC3B genes in the plasma of CRC patients [19]. Additionally, we have registered a high frequency of the HIC1 hypermethylation in the plasma of CRC pa- tients – 80 % (8/10). Similar study of the healthy do- nor’s plasma has revealed the hypermethylation of HIC1 at the similar level – 80 % (12/15). No difference in the HIC1 and COL2A1 hypermethylation was observed in CRC patients and healthy donors: mean values of CtCRC 32.7 – HIC1 and 28.6 – COL2A1 and Cthealthy donors 35.0 – HIC1 and 30.5 – COL2A1. This indicates a low selectivity of the HIC1 hyper- methylation in CRC patients. Therefore, we concluded that the HIC1 hypermethylation is not a valuable mar- ker for the prediction of CRC. We proposed that a two-stage verification must be applied for CRC screening. These stages include the measurement of the cell-free circulating DNA and the following detection of the methylated fragments of APC, FHIT, and LRRC3B genes in the CRC patient plas- ma. This allows us to achieve a sensitivity of the panel in CRC detection up to 75 % (Table 2). However, our research has not resulted in the sen- sitivity of 100 % for the CRC registration that is essen- tial for the prevention of this disease. We hope that a hi- gher sensitivity might be achieved by further extension of the gene panel for the identification of methylated DNA in the plasma of CRC patients. Conclusions. In the present work we have charac- terized hypermethylation of the APC, FHIT, LRRC3B, and HIC1 genes in the patients with CRC in compari- son with the healthy donors. We have found that hyper- methylation of the APC, FHIT, and LRRC3B gene frag- ments in the plasma fully corresponds to hypermethy- lation of these genes in the tumors. We have proposed and tested the novel approach for CRC screening, based on the detection of cell-free DNA and methylated fragments of the well-known tu- mor associated genes, such as APC, FHIT, LRRC3B, and HIC1 in the blood plasma. With such approach 75 % of sensitivity could be achieved. The sensitivity for CRC detection might be increased by the analysis of additio- nal tumor-associated genes. Funding. This work was supported by a grant from the Ukrainian Academy of Sciences (41/12). Ïîð³âíÿëüíèé àíàë³ç åï³ãåíåòè÷íèõ ìàðêåð³â ó ïëàçì³ êðîâ³ ïàö³ºíò³â, õâîðèõ íà ðàê òîâñòîãî êèøå÷íèêà Î. Ã. Êîíäðàòîâ, Ê. À. Íåêðàñîâ, Ë. Â. Ëîòîöüêà, Ã. Â. Ïàíàñåíêî, Ë. À. Ñòîëÿð, Þ. Â. Ëàïñüêà, Î. Î. Êîëåñíèê, ². Á. Ùåïîò³í, À. Â. Ðèíäè÷, Â. ². Êàøóáà Ðåçþìå Ìåòà. Ðîçðîáêà ìåíø ³íâàçèâíèõ ìåòîäèê äëÿ ñêðèí³íãó çëîÿê³ñ- íèõ ïóõëèí òîâñòîãî êèøå÷íèêà (CRC). Ìåòîäè. Âèêîðèñòàíî ê³ëüê³ñíó ÏËÐ ³ ìåòèë-ñïåöèô³÷íó ÏËÐ. Ðåçóëüòàòè. Ïîêàçàíî, ùî ñåðåäíº çíà÷åííÿ êîíöåíòðàö³é â³ëüíî öèðêóëþþ÷î¿ ÄÍÊ ó ïëàçì³ êðîâ³ º ñòàòèñòè÷íî äîñòîâ³ðíî âèùèì ó ïàö³ºíò³â ç CRC ïîð³âíÿíî ç³ çäîðîâèìè äîíîðàìè (p < 0,01). Âñòàíîâëåíî ã³ïåðìå- òèëþâàííÿ ãåí³â APC, FHIT, LRRC3B ³ HIC1 ó ïóõëèíàõ òà ïëàçì³ õâîðèõ íà CRC. Âèñíîâêè. Íàìè çàïðîïîíîâàíî ³ ïåðåâ³ðåíî íîâ³ò- í³é ï³äõ³ä äëÿ ñêðèí³íãó CRC, ÿêèé áàçóºòüñÿ íà âèçíà÷åíí³ ïîçà- êë³òèííî¿ ÄÍÊ ³ ìåòèëüîâàíèõ ôðàãìåíò³â ÄÍÊ ó ïëàçì³. Êëþ÷îâ³ ñëîâà: çëîÿê³ñí³ ïóõëèíè òîâñòîãî êèøå÷íèêà, â³ëüíî öèðêóëþþ÷à ÄÍÊ, ìåòèëþâàííÿ ÄÍÊ, APC, FHIT, LRRC3B, HIC1. Ñðàâíèòåëüíûé àíàëèç ýïèãåíåòè÷åñêèõ ìàðêåðîâ â ïëàçìå êðîâè ïàöèåíòîâ, áîëüíûõ ðàêîì òîëñòîãî êèøå÷íèêà À. Ã. Êîíäðàòîâ, Ê. À. Íåêðàñîâ, Ë. Â. Ëîòîöêàÿ, Ã. Â. Ïàíàñåíêî, Ë. À. Ñòîëÿð, Þ. Â. Ëàïñêàÿ, Î. Î. Êîëåñíèê, È. Á. Ùåïîòèí, À. Â. Ðûíäè÷, Â. È. Êàøóáà Ðåçþìå Öåëü. Ðàçðàáîòêà ìåíåå èíâàçèâíûõ ìåòîäèê äëÿ ñêðèíèíãà çëîêà- ÷åñòâåííûõ îïóõîëåé òîëñòîãî êèøå÷íèêà (CRC). Ìåòîäû. Èñ- ïîëüçîâàíà êîëè÷åñòâåííàÿ ÏÖÐ è ìåòèë-ñïåöèôè÷åñêàÿ ÏÖÐ. Ðåçóëüòàòû. Ïîêàçàíî, ÷òî ñðåäíåå çíà÷åíèå ñâîáîäíî öèðêóëè- ðóþùåé ÄÍÊ â ïëàçìå ñòàòèñòè÷åñêè äîñòîâåðíî âûøå ó ïàöè- 133 COMPARATIVE ANALYSIS OF EPIGENETIC MARKERS OF PATIENTS WITH COLORECTAL CANCER åíòîâ ñ CRC ïî ñðàâíåíèþ ñî çäîðîâûìè äîíîðàìè (p < 0,01). Óñòàíîâëåíî ãèïåðìåòèëèðîâàíèå ãåíîâ APC, FHIT, LRRC3B è HIC1â îïóõîëÿõ è ïëàçìå ïàöèåíòîâ ñ CRC. Âûâîäû. Íàìè ïðåäëî- æåí è ïðîâåðåí íîâåéøèé ïîäõîä äëÿ ñêðèíèíãà CRC, áàçèðóþ- ùèéñÿ íà îïðåäåëåíèè âíåêëåòî÷íîé ÄÍÊ è ìåòèëèðîâàííûõ ôðàã- ìåíòîâ ÄÍÊ â ïëàçìå. Êëþ÷åâûå ñëîâà: çëîêà÷åñòâåííûå îïóõîëè òîëñòîãî êèøå÷- íèêà, ñâîáîäíî öèðêóëèðóþùàÿ ÄÍÊ, ìåòèëèðîâàííàÿ ÄÍÊ, APC, FHIT, LRRC3B, HIC1. REFERENCES 1. Ferlay J, Shin HR, Bray F, Forman D, Mathers C, Parkin DM. Estimates of worldwide burden of cancer in 2008: GLOBOCAN 2008. Int J Cancer. 2010; 127(12):2893–917. 2. Rex DK, Bond JH, Winawer S, Levin TR, Burt RW, Johnson DA, Kirk LM, Litlin S, Lieberman DA, Waye JD, Church J, Marshall JB, Riddell RH; U.S. Multi-Society Task Force on Colorectal Cancer. Quality in the technical performance of colonoscopy and the continuous quality improvement process for colonoscopy: recommendations of the U.S. Multi-Society Task Force on Colo- rectal Cancer. Am J Gastroenterol. 2002; 97(6):1296–308. 3. Louis MA, Nandipati K, Astorga R, Mandava A, Rousseau CP, Mandava N. Correlation between preoperative endoscopic and intraoperative findings in localizing colorectal lesions. World J Surg. 2010; 34(7):1587–91. 4. Bird A. DNA methylation patterns and epigenetic memory. Genes Dev. 2002; 16(1):6–21. 5. Esteller M. CpG island hypermethylation and tumor suppressor genes: a booming present, a brighter future. Oncogene. 2002; 21(35):5427–40. 6. Kohler C, Barekati Z, Radpour R, Zhong XY. Cell-free DNA in the circulation as a potential cancer biomarker. Anticancer Res. 2011; 31(8):2623–8. 7. Kim M, Kim JH, Jang HR, Kim HM, Lee CW, Noh SM, Song KS, Cho JS, Jeong HY, Hahn Y, Yeom YI, Yoo HS, Kim YS. LRRC3B, encoding a leucine-rich repeat-containing protein, is a putative tumor suppressor gene in gastriccancer. Cancer Res. 2008; 68(17):7147–55. 8. Pichiorri F, Palumbo T, Suh SS, Okamura H, Trapasso F, Ishii H, Huebner K, Croce CM. Fhit tumor suppressor: guardian of the preneoplastic genome. Future Oncol. 2008; 4(6):815–24. 9. Dumitrescu RG. Epigenetic markers of early tumor develop- ment. Methods Mol Biol. 2012; 863:3–14. 10. Dehennaut V, Leprince D. Implication of HIC1 (Hypermethyla- ted In Cancer 1) in the DNA damage response. Bull Cancer. 2009; 96(11):E66–72. 11. Kondratov AG, Stoliar LA, Kvasha SM, Gordiyuk VV, Zgonnyk YM, Gerashchenko AV, Vozianov AF, Rynditch AV, Zabarovsky ER, Kashuba VI. Methylation pattern of the putative tumor-sup- pressor gene LRRC3B promoter in clear cell renal cell carcino- mas. Mol Med Rep. 2012; 5(2):509–12. 12. Li B, Wang B, Niu LJ, Jiang L, Qiu CC. Hypermethylation of multiple tumor-related genes associated with DNMT3b up-regu- lation served as a biomarker for early diagnosis of esophageal squamous cell carcinoma. Epigenetics. 2011; 6(3):307–16. 13. Kvasha S, Gordiyuk V, Kondratov A, Ugryn D, Zgonnyk YM, Rynditch AV, Vozianov AF. Hypermethylation of the 5'CpG is- land of the FHIT gene in clear cell renal carcinomas. Cancer Lett. 2008; 265(2):250–7. 14. Kristensen LS, Raynor MP, Candiloro I, Dobrovic A. Methyla- tion profiling of normal individuals reveals mosaic promoter me- thylation of cancer-associated genes. Oncotarget. 2012; 3(4): 450–61. 15. Segditsas S, Sieber OM, Rowan A, Setien F, Neale K, Phillips RK, Ward R, Esteller M, Tomlinson IP. Promoter hypermethylation leads to decreased APC mRNA expression in familial polyposis and sporadic colorectal tumours, but does not substitute for trun- cating mutations. Exp Mol Pathol. 2008; 85(3):201–6. 16. Sinha R, Hussain S, Mehrotra R, Kumar RS, Kumar K, Pande P, Doval DC, Basir SF, Bharadwaj M. Kras gene mutation and RASSF1A, FHIT and MGMT gene promoter hypermethylation: indicators of tumor staging and metastasis in adenocarcinoma- tous sporadic colorectal cancer in Indian population. PLoS One. 2013; 8(4):e60142. 17. Tian XQ, Zhang Y, Sun D, Zhao S, Xiong H, Fang J. Epigenetic silencing of LRRC3B in colorectal cancer. Scand J Gastroente- rol. 2009; 44(1):79–84. 18. Abouzeid HE, Kassem AM, Abdel Wahab AH, El-mezayen HA, Sharad H, Abdel Rahman S. Promoter hypermethylation of RAS SF1A, MGMT, and HIC-1 genes in benign and malignant colo- rectal tumors. Tumour Biol. 2011; 32(5):845–52. 19. Skrypkina IYa, Kondratov OG, Tsyba LO, Panasenko GV, Ni- kolaienko OV, Romanenko AM, Kolesnyk OO, Morderer DYe, Nekrasov KA, Kashuba VI, Vozianov SO, Shchepotin IB, Ryn- ditch AV. Detection of cell-free DNA and gene-specific methy- lation in blood plasma of patients with renal and colon cancer. Science and Innovation. 2012; 8(6):60–6. Received 28.08.13 134 KONDRATOV A. G. ET AL.